نتایج جستجو برای: survival motor neuron gene

تعداد نتایج: 1595196  

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2006
Chen Lai Chengsong Xie Stefanie G McCormack Hsueh-Cheng Chiang Marta K Michalak Xian Lin Jayanth Chandran Hoon Shim Mika Shimoji Mark R Cookson Richard L Huganir Jeffrey D Rothstein Donald L Price Philip C Wong Lee J Martin J Julius Zhu Huaibin Cai

Amyotrophic lateral sclerosis (ALS), the most common adult-onset motor neuron disease is caused by a selective loss of motor neurons. One form of juvenile onset autosomal recessive ALS (ALS2) has been linked to the loss of function of the ALS2 gene. The pathogenic mechanism of ALS2-deficiency, however, remains unclear. To further understand the function of alsin that is encoded by the full-leng...

Journal: :Turkish Journal of Pediatrics 2021

Background Amyotrophic lateral sclerosis (ALS) is a chronic motor neuron disease characterised by progressive weakness in striated muscles resulting from the destruction of neuronal cells. The term juvenile ALS (JALS) used for patients whose symptoms start before 25 years age. JALS may be sporadic or familial. Case Here, we present case because its rarity children. heterozygous p.Pro525Leu (c.1...

Journal: :The Journal of clinical investigation 2011
Kathryn J Swoboda

Spinal muscular atrophy (SMA) is an autosomal recessive neurodegenerative disease that predominantly affects motor neurons, resulting in progressive muscular atrophy and weakness. SMA arises due to insufficient survival motor neuron (SMN) protein levels as a result of homozygous disruption of the SMN1 gene. SMN upregulation is a promising and potent treatment strategy for this currently incurab...

2013
Justin G. Boyer Andrew Ferrier Rashmi Kothary

Spinal muscular atrophy (SMA), amyotrophic lateral sclerosis (ALS), and spinal-bulbar muscular atrophy (SBMA) are devastating diseases characterized by the degeneration of motor neurons. Although the molecular causes underlying these diseases differ, recent findings have highlighted the contribution of intrinsic skeletal muscle defects in motor neuron diseases. The use of cell culture and anima...

Journal: :Journal of neurology, neurosurgery, and psychiatry 2003
M R Turner M J Parton C E Shaw P N Leigh A Al-Chalabi

Motor neuron disease is a clinically heterogeneous disease with significant differences in survival. The authors have characterised a subset of long term survivors seen in a tertiary clinic over a 12 year period in terms of clinical variables and demographics, comparing them with short term survivors and the remaining population. Thirty of 769 patients survived more than 10 years, corresponding...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 1995
L J Richards M Murphy R Dutton T J Kilpatrick A C Puche B Key S S Tan P S Talman P F Bartlett

We have investigated the differentiation potential of precursor cells within the developing spinal cord of mice and have shown that spinal cord cells from embryonic day 10 specifically give rise to neurons when plated onto an astrocytic monolayer, Ast-1. These neurons had the morphology of motor neurons and > 83% expressed the motor neuron markers choline acetyltransferase, peripherin, calciton...

Journal: :iranian journal of neurology 0
majid ghasemi department of neurology, isfahan neuroscience research center, isfahan university of medical sciences, isfahan, iran. farzad fatehi department of neurology, shariati hospital, iranian center of neurological research, tehran university of medical sciences, tehran, iran bahador asadi aja university of medical sciences, tehran, iran fariborz khorvash department of neurology, isfahan neuroscience research center, isfahan university of medical sciences, isfahan, iran

amyotrophic lateral sclerosis (als), the most common form of motor neuron disease, is a progressive and devastating disease involving both lower and upper motor neurons, typically following a relentless progression towards death. therefore, all efforts must be made by the clinician to exclude alternative and more treatable entities. als with laboratory abnormalities of uncertain significance is...

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 1998
A G Estévez N Spear S M Manuel R Radi C E Henderson L Barbeito J S Beckman

Primary cultures of rat embryonic motor neurons deprived of brain-derived neurotrophic factor (BDNF) induce neuronal nitric oxide synthase (NOS) within 18 hr. Subsequently, >60% of the neurons undergo apoptosis between 18 and 24 hr after plating. Nitro-L-arginine and nitro-L-arginine methyl ester (L-NAME) prevented motor neuron death induced by trophic factor deprivation. Exogenous generation o...

2011
Anindya Sen Takakazu Yokokura Mark W. Kankel Douglas N. Dimlich Jan Manent Subhabrata Sanyal Spyros Artavanis-Tsakonas

Spinal muscular atrophy (SMA), a devastating neurodegenerative disorder characterized by motor neuron loss and muscle atrophy, has been linked to mutations in the Survival Motor Neuron (SMN) gene. Based on an SMA model we developed in Drosophila, which displays features that are analogous to the human pathology and vertebrate SMA models, we functionally linked the fibroblast growth factor (FGF)...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید