نتایج جستجو برای: scn1a mutations

تعداد نتایج: 173129  

2003
ANDRE HENRIQUES

It is well-known that an effective orbifold M (one for which the local stabilizer groups act effectively) can be presented as a quotient of a smooth manifold P by a locally free action of a compact lie group K. We use the language of groupoids to provide a partial answer to the question of whether a noneffective orbifold can be so presented. We also note some connections to stacks and gerbes.

Journal: :Seizure 2009
Krista Mahoney Susan J. Moore David Buckley Muhammed Alam Patrick Parfrey Sharon Penney Nancy Merner Kathy Hodgkinson Terry-Lynn Young

PURPOSE To describe the spectrum of clinical disease in a mutliplex family with an autosomal dominant form of generalized epilepsy with febrile seizures plus (GEFS+) and determine its genetic etiology. METHODS Medical and family history was obtained on 11 clinically affected individuals and their relatives across three generations through medical chart review and home visits. A candidate gene...

Journal: :Annals of neurology 2013
Yu Liu Luis F Lopez-Santiago Yukun Yuan Julie M Jones Helen Zhang Heather A O'Malley Gustavo A Patino Janelle E O'Brien Raffaella Rusconi Ajay Gupta Robert C Thompson Marvin R Natowicz Miriam H Meisler Lori L Isom Jack M Parent

OBJECTIVE Neuronal channelopathies cause brain disorders, including epilepsy, migraine, and ataxia. Despite the development of mouse models, pathophysiological mechanisms for these disorders remain uncertain. One particularly devastating channelopathy is Dravet syndrome (DS), a severe childhood epilepsy typically caused by de novo dominant mutations in the SCN1A gene encoding the voltage-gated ...

پایان نامه :وزارت علوم، تحقیقات و فناوری - پژوهشگاه ملی مهندسی ژنتیک وزیست فناوری - دانشکده پزشکی 1389

تشنج عارضه شایعی است که بدلیل اختلال در مسیر انتقال پیام در سلول های عصبی یا نرون های مغزی رخ داده وعلل گسترده ای برای آن متصور است. ادامه حملات تشنجی منجر به بیماری صرع گردیده که شیوعی بین 1-3 درصد در جوامع مختلف دارد. گروهی از حملات صرعی بدون دلیل مشخص به دنبال تب یا بدون تب رخ داده، پیشرونده هستند و به درمان داروئی پاسخ نشان نمی دهند. علت نامشخص،تنوع در شدت و نوع بالینی، عوارض و پیامدهای شدی...

Journal: :Egyptian Journal of Medical Human Genetics 2021

Abstract Background Epilepsy is one of the most common and heterogeneous neurological diseases. The main clinical signs disease are repeated symptomatic or idiopathic epileptic seizures both convulsive non-convulsive nature that develop against a background lost preserved consciousness. genetic component plays large role in etiology forms epilepsy. study molecular basis disorders has led to rap...

2016
C. Peters R. E. Rosch E. Hughes P. C. Ruben

Dravet syndrome is the prototype of SCN1A-mutation associated epilepsies. It is characterised by prolonged seizures, typically provoked by fever. We describe the evaluation of an SCN1A mutation in a child with early-onset temperature-sensitive seizures. The patient carries a heterozygous missense variant (c3818C > T; pAla1273Val) in the NaV1.1 brain sodium channel. We compared the functional ef...

2015
Yifan Zhang Angéla Kecskés Daniëlle Copmans Mélanie Langlois Alexander D. Crawford Berten Ceulemans Lieven Lagae Peter A. M. de Witte Camila V. Esguerra

Dravet syndrome (DS) is one of the most pharmacoresistant and devastating forms of childhood epilepsy syndromes. Distinct de novo mutations in the SCN1A gene are responsible for over 80% of DS cases. While DS is largely resistant to treatment with existing anti-epileptic drugs, promising results have been obtained in clinical trials with human patients treated with the serotonin agonist fenflur...

Journal: :Brain : a journal of neurology 2012
A Brunklaus R Ellis E Reavey G H Forbes S M Zuberi

Dravet syndrome is a severe infantile onset epileptic encephalopathy associated with mutations in the sodium channel alpha 1 subunit gene SCN1A. To date no large studies have systematically examined the prognostic, clinical and demographic features of the disease. We prospectively collected data on a UK cohort of individuals with Dravet syndrome during a 5-year study period and analysed demogra...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید