نتایج جستجو برای: fshd

تعداد نتایج: 347  

2012
Yen-Mou Lu Yi-Jing Lue

This chapter places emphasis on patients with more weakness in proximal than distal parts. The most common type of proximal muscular dystrophy is Duchenne muscular dystrophy (DMD). Due to rapid deterioration, DMD can be seen as a severe form of muscular dystrophy. Other types of proximal muscular dystrophies have a slower rate of disease progression compared to DMD, such as Beck muscular dystro...

2014
Libby Wood Teresinha Evangelista Fiona Norwood Richard Orrell Marita Pohlschmidt Mark Busby Andrew Graham David Hilton-Jones Cheryl Longman Peter Lunt Mark Roberts Stuart Watt Suzanne Watt Tracey Willis Hanns Lochmüller

The United Kingdom (UK) Facioscapulohumeral Dystrophy (FSHD) Patient Registry launched in May 2013. Funded by the Muscular Dystrophy Campaign and supported by the TREAT-NMD Alliance. This patient driven registry collects the internationally agreed core dataset, an outcome of an ENMC Workshop held in 2010 [1], through a novel online portal (http://www.fshd-registry. org/uk). Genetic details are ...

Journal: :Molecules 2015
Sachchida Nand Pandey Hunain Khawaja Yi-Wen Chen

Facioscapulohumeral muscular dystrophy (FSHD) is believed to be caused by aberrant expression of double homeobox 4 (DUX4) due to epigenetic changes of the D4Z4 region at chromosome 4q35. Detecting DUX4 is challenging due to its stochastic expression pattern and low transcription level. In this study, we examined different cDNA synthesis strategies and the sensitivity for DUX4 detection. In addi...

2009
Darko Bosnakovski Randy S. Daughters Zhaohui Xu Jonathan M. W. Slack Michael Kyba

Facioscapulohumeral muscular dystrophy (FSHD) is caused by contractions of D4Z4 repeats at 4q35.2 thought to induce misregulation of nearby genes, one of which, DUX4, is actually localized within each repeat. A conserved ORF (mDUX), embedded within D4Z4-like repeats, encoding a double-homeodomain protein, was recently identified on mouse chromosome 10. We show here that high level mDUX expressi...

Journal: :PloS one 2016
Abhijit Dandapat Benjamin J Perrin Christine Cabelka Maria Razzoli James M Ervasti Alessandro Bartolomucci Dawn A Lowe Michael Kyba

Facioscapulohumeral muscular dystrophy (FSHD) is caused by mutations leading to ectopic expression of the transcription factor DUX4, and encompasses both muscle-related and non-muscle phenotypes. Mouse models bearing this gene represent valuable tools to investigate which pathologies are due to DUX4 expression, and how DUX4 leads to these pathologies. The iDUX4(2.7) mouse contains an X-linked d...

2016
Paul Knopp Yvonne D Krom Christopher R S Banerji Maryna Panamarova Louise A Moyle Bianca den Hamer Silvère M van der Maarel Peter S Zammit

Skeletal muscle wasting in facioscapulohumeral muscular dystrophy (FSHD) results in substantial morbidity. On a disease-permissive chromosome 4qA haplotype, genomic and/or epigenetic changes at the D4Z4 macrosatellite repeat allows transcription of the DUX4 retrogene. Analysing transgenic mice carrying a human D4Z4 genomic locus from an FSHD-affected individual showed that DUX4 was transiently ...

2012
Stanley S. Lefkowitz Doris L. Lefkowitz Jeremy Kethley

BACKGROUND Facioscapulohumeral muscular dystrophy (FSHD) is the 3(rd) most common form of muscular dystrophy. Effective treatments for any of the muscular dystrophies have yet to be realized. This report describes such a treatment. CASE REPORT A 66 year old female was diagnosed with osteoporosis. She had been diagnosed with FSHD muscular dystrophy a number of years previously by both genetic ...

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