نتایج جستجو برای: 46xy dsd

تعداد نتایج: 1104  

Journal: :The Journal of the Association of Physicians of India 2008
Usha Kini G Bantwal V Ayyar Jyothi Idiculla

Ovotesticular DSD is not an uncommon disorder. The presence of Y chromosome confers a high risk of neoplastic transformation in dysgenetic gonads. The neoplastic development in these patients is associated with the presence of Y chromosome and intra abdominal location of the abnormal gonad. We report histogenetic details of a rare occurrence of bilateral gonadoblastomas and left sided dysgermin...

Journal: :Sexual development : genetics, molecular biology, evolution, endocrinology, embryology, and pathology of sex determination and differentiation 2016
Anu Bashamboo Ken McElreavey

In this review we will consider the gene mutations responsible for the non-syndromic forms of disorders of sex development (DSD) and how recent genetic findings are providing insights into the mechanism of sex determination. High-throughput sequencing technologies are having a major impact on our understanding of the genetic basis of rare human disorders, including DSD. The study of human DSD i...

Journal: :Journal of pediatric urology 2012
Lyn S Chitty Pierre Chatelain Katja P Wolffenbuttel Yves Aigrain

Disorders of sex development (DSD) rarely present prenatally but, as they are very complex conditions, management should be directed by highly specialised medical teams to allow consideration of all aspects of diagnosis, treatment and ethical issues. In this brief review, we present an overview of the prenatal presentation and management of DSD, including the sonographic appearance of normal ge...

2000
Kam-yiu Lam Gary C.K. Law Victor C.S. Lee

A Distributed Real-time Active Database System (DRTADBS) reacts to the critical events occurred in the external environment by triggering of transactions. In this paper, the priority and deadline assignment to triggered transactions under two coupling modes, the deferred and immediate, in a DRTADBS is discussed. Two new approaches, the data state dependent (DSD) and the transaction-data deadlin...

2012
Kalum T. Wettasinghe Nirmala D. Sirisena Prabha H. Andraweera Rohan W. Jayasekara Vajira H. W. Dissanayake

Ovotesticular disorder of sex development (OT-DSD) is a rare disorder of sexual differentiation in which the gonads of an individual are characterized by the presence of both mature ovarian and testicular tissues. The objective of this paper is to report the clinical, cytogenetic and histopathological findings in Sri Lankan patients diagnosed with OT-DSD who were referred to the Human Genetics ...

2012
A. Zulfa Juniarto Yvonne G. van der Zwan Ardy Santosa Remko Hersmus Frank H. de Jong Renske Olmer Hennie T. Bruggenwirth Axel P. N. Themmen Katja P. Wolffenbuttel Leendert H. J. Looijenga Sultana M. H. Faradz Stenvert L. S. Drop

Disorder of sex development (DSD) patients in Indonesia most often do not receive a proper diagnostic evaluation and treatment. This study intended to categorize 88 Indonesian patients in accordance with the new consensus DSD algorithm. Diagnostic evaluation including clinical, hormonal, genetic, imaging, surgical, and histological parameters was performed. Fifty-three patients were raised as m...

2009
Biagio Zuccarello Antonella Spada Antonio Centorrino Nunzio Turiaco Maria Rosaria Chirico Saveria Parisi

Background/Purpose. Kimura's diamond-shaped-duodenoduodenostomy (DSD) is a known technique for the correction of congenital intrinsic duodenal obstruction. We present a modification of the technique and review the advantages of this new technique. Methods. From 1992 to 2006, 14 newborns were treated for duodenal atresia. We inverted the direction of the duodenal incisions: a longitudinal incisi...

Journal: :Clinical genetics 2013
V A Arboleda H Lee F J Sánchez E C Délot D E Sandberg W W Grody S F Nelson E Vilain

Disorders of sex development (DSD) are rare disorders in which there is discordance between chromosomal, gonadal, and phenotypic sex. Only a minority of patients clinically diagnosed with DSD obtains a molecular diagnosis, leaving a large gap in our understanding of the prevalence, management, and outcomes in affected patients. We created a novel DSD-genetic diagnostic tool, in which sex develo...

2016
N. C. Hornig M. Ukat H. U. Schweikert O. Hiort R. Werner S. L. S. Drop M. Cools I. A. Hughes L. Audi S. F. Ahmed J. Demiri P. Rodens L. Worch G. Wehner A. E. Kulle D. Dunstheimer E. Müller-Roßberg T. Reinehr A. T. Hadidi A. K. Eckstein C. van der Horst C. Seif R. Siebert O. Ammerpohl P.-M. Holterhus

CONTEXT Only approximately 85% of patients with a clinical diagnosis complete androgen insensitivity syndrome and less than 30% with partial androgen insensitivity syndrome can be explained by inactivating mutations in the androgen receptor (AR) gene. OBJECTIVE The objective of the study was to clarify this discrepancy by in vitro determination of AR transcriptional activity in individuals wi...

2018
Karen M Rothacker Katie L Ayers Dave Tang Kiranjit Joshi Jocelyn A van den Bergen Gorjana Robevska Naeem Samnakay Lakshmi Nagarajan Kate Francis Andrew H Sinclair Catherine S Choong

Background Desert hedgehog (DHH) mutations have been described in only a limited number of individuals with 46, XY disorders of sex development (DSD) presenting as either partial or complete gonadal dysgenesis. Gonadal tumours and peripheral neuropathy have been associated with DHH mutations. Herein we report a novel, homozygous mutation of DHH identified through a targeted, massively parallel ...

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