نتایج جستجو برای: chromosome microdeletion

تعداد نتایج: 120218  

2009
Seong Kwan Jung Kyu Hee Park Hae Kyung Shin Hee Eun Baik-Lin Eun Kee Hwan Yoo Young Sook Hong Joo Won Lee Sook Young Bae

SmithMagenis syndrome (SMS) is a rare disorder with multiple congenital anomalies caused by a heterozygous interstitial deletion involving chromosome 17p11.2, where the retinoic acid-induced 1 (RAI1) gene is located, or by a mutation of RAI1. Approximately 90% of the patients with SMS have a detectable 17p11.2 microdeletion on fluorescence in-situ hybridization (FISH). SMS is characterized by m...

2013
Adrian Zammit Deborah Grech Marguerat Josephine Psaila Alexander Attard

Introduction. DiGeorge syndrome is a developmental defect commonly caused by a microdeletion on the long arm of chromosome 22 or less frequently by a deletion of the short arm of chromosome 10. Case report. We report a case of a gentleman with mild dysmorphic features who presented with hypocalcaemia-induced seizures and an associated thyroid mass with a background of learning difficulties and ...

2015
Adrian Mc Cormack Cynthia Sharpe Nerine Gregersen Warwick Smith Ian Hayes Alice M. George Donald R. Love

To date, there have been only a few reports of patients carrying a microdeletion in chromosome 12q14. These patients usually present with pre- and postnatal growth retardation, and developmental delay. Here we report on two additional patients with both genotype and phenotype differences. Similar to previously published cases, one patient has haploinsufficiency of the HMGA2 gene and shows sever...

Journal: :American journal of medical genetics. Part A 2010
Ana Cristina V Krepischi Carla Rosenberg Silvia S Costa John A Crolla Shuwen Huang Angela M Vianna-Morgante

A Novel De Novo Microdeletion Spanning the SYNGAP1 Gene on the Short Arm of Chromosome 6 Associated With Mental Retardation Ana Cristina V. Krepischi, Carla Rosenberg, Silvia S. Costa, John A. Crolla, Shuwen Huang, and Angela M. Vianna-Morgante* Department of Genetics and Evolutionary Biology, Institute of Biosciences, University of S~ao Paulo, S~ao Paulo, Brazil AC Camargo Cancer Hospital, S~a...

2014
Shujuan Jiang Jiubin Zhang Dan Huang Yuanyuan Zhang Xiaoliang Liu Yinzhao Wang Rong He Yanyan Zhao

Nail patella syndrome (NPS) is an autosomal dominant disorder characterized by nail malformations, patellar apoplasia, or patellar hypoplasia. Mutations within the LMX1B gene are found in 85% of families with NPS; thus, this gene has been characterized as the causative gene of NPS. In this study, we identified a heterozygous microdeletion of the entire LMX1B gene using multiplex ligation-depend...

2013
Sira Korpaisarn Objoon Trachoo Chutintorn Sriphrapradang

We report a 26-year-old Thai man who presented with hypoparathyroidism in adulthood. He had no history of cardiac disease and recurrent infection. His subtle dysmorphic facial features and mild intellectual impairment were suspected for chromosome 22q11.2 deletion syndrome. The diagnosis was confirmed by fluorescence in situ hybridization, which found microdeletion in 22q11.2 region. The charac...

Journal: :American journal of medical genetics. Part A 2003
Joan H M Knoll Peter K Rogan

We developed single copy probes from the draft genome sequence for fluorescence in situ hybridization (scFISH) which precisely delineate chromosome abnormalities at a resolution equivalent to genomic Southern analysis. This study illustrates how scFISH probes detect cryptic and subtle abnormalities and localize the sites of chromosome rearrangements. scFISH probes are substantially shorter than...

Journal: :Journal of medical genetics 1992
I Cross J Delhanty P Chapman L V Bowles D Griffin J Wolstenholme M Bradburn J Brown C Wood A Gunn

We report familial adenomatous polyposis coli (FAPC) with epidermoid cysts, osteomata, and areas of congenital hypertrophy of the retinal pigment epithelium (CHRPEs) in a male patient and his maternal aunt, both of whom suffered a mild to moderate degree of mental handicap. Both had an interstitial deletion of the long arm of chromosome 5 (del(5)(q22q23.2)). Two other normal family members had ...

Journal: :Genome research 2016
Kiana Mohajeri Stuart Cantsilieris John Huddleston Bradley J Nelson Bradley P Coe Catarina D Campbell Carl Baker Lana Harshman Katherine M Munson Zev N Kronenberg Milinn Kremitzki Archana Raja Claudia Rita Catacchio Tina A Graves Richard K Wilson Mario Ventura Evan E Eichler

Recurrent rearrangements of Chromosome 8p23.1 are associated with congenital heart defects and developmental delay. The complexity of this region has led to inconsistencies in the current reference assembly, confounding studies of genetic variation. Using comparative sequence-based approaches, we generated a high-quality 6.3-Mbp alternate reference assembly of an inverted Chromosome 8p23.1 hapl...

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