نتایج جستجو برای: β globin gene cluster region

تعداد نتایج: 1892840  

Journal: :Clinical chemistry 2012
Kwan-Wood G Lam Peiyong Jiang Gary J W Liao K C Allen Chan Tak Y Leung Rossa W K Chiu Y M Dennis Lo

BACKGROUND A genomewide genetic and mutational profile of a fetus was recently determined via deep sequencing of maternal plasma DNA. This technology could have important applications for noninvasive prenatal diagnosis (NIPD) of many monogenic diseases. Relative haplotype dosage (RHDO) analysis, a core step of this procedure, would allow one to elucidate the maternally inherited half of the fet...

2012
Ivan Junier Ryan K. Dale Chunhui Hou François Képès Ann Dean

The principles underlying the architectural landscape of chromatin beyond the nucleosome level in living cells remains largely unknown despite its potential to play a role in mammalian gene regulation. We investigated the three-dimensional folding of a 1 Mbp region of human chromosome 11 containing the β-globin genes by integrating looping interactions of the CCCTC-binding insulator protein CTC...

Journal: :Molecular cell 2016
Caroline R Bartman Sarah C Hsu Chris C-S Hsiung Arjun Raj Gerd A Blobel

Mammalian genes transcribe RNA not continuously, but in bursts. Transcriptional output can be modulated by altering burst fraction or burst size, but how regulatory elements control bursting parameters remains unclear. Single-molecule RNA FISH experiments revealed that the β-globin enhancer (LCR) predominantly augments transcriptional burst fraction of the β-globin gene with modest stimulation ...

2003
Claudine Lapoumeroulie Guy Trabuchet Moshe Mittelman Rajagopal Krishnamoorthy

The clinical diversity of sickle cell anemia is strongly related to the degree of intracellular hemoglobin S (Hb S) polymerization, which in turn is dependent on the intracellular concentration of Hb S. We have recently defined a region of DNA approximately 500 bp 5‘ to the human p-globin gene that acts as a silencer for the transcription of this gene and have shown that a polymbrphism in this ...

Journal: :Haematologica 2015
Stefano Rivella

β-thalassemias are monogenic disorders characterized by defective synthesis of the β-globin chain, one of the major components of adult hemoglobin. A large number of mutations in the β-globin gene or its regulatory elements have been associated with β-thalassemias. Due to the complexity of the regulation of the β-globin gene and the role of red cells in many physiological processes, patients ca...

Journal: :The New England journal of medicine 2017
Jean-Antoine Ribeil Salima Hacein-Bey-Abina Emmanuel Payen Alessandra Magnani Michaela Semeraro Elisa Magrin Laure Caccavelli Benedicte Neven Philippe Bourget Wassim El Nemer Pablo Bartolucci Leslie Weber Hervé Puy Jean-François Meritet David Grevent Yves Beuzard Stany Chrétien Thibaud Lefebvre Robert W Ross Olivier Negre Gabor Veres Laura Sandler Sandeep Soni Mariane de Montalembert Stéphane Blanche Philippe Leboulch Marina Cavazzana

Sickle cell disease results from a homozygous missense mutation in the β-globin gene that causes polymerization of hemoglobin S. Gene therapy for patients with this disorder is complicated by the complex cellular abnormalities and challenges in achieving effective, persistent inhibition of polymerization of hemoglobin S. We describe our first patient treated with lentiviral vector-mediated addi...

Journal: :Haematologica 2014
Guanheng Yang Wansheng Shi Xingyin Hu Jingzhi Zhang Zhijuan Gong Xinbing Guo Zhaorui Ren Fanyi Zeng

Although β-thalassemia is one of the most common human genetic diseases, there is still no effective treatment other than bone marrow transplantation. Induced pluripotent stem cells have been considered good candidates for the future repair or replacement of malfunctioning organs. As a basis for developing transgenic induced pluripotent stem cell therapies for thalassemia, β(654) induced plurip...

Journal: :Blood 1993
J A Sharpe R J Summerhill P Vyas G Gourdon D R Higgs W G Wood

Erythroid-specific DNase 1 hypersensitive sites have been identified at the promoters of the human alpha-like genes and within the region from 4 to 40 kb upstream of the gene cluster. One of these sites, HS-40, has been shown previously to be the major regulator of tissue-specific alpha-globin gene expression. We have now examined the function of other hypersensitive sites by studying the expre...

Journal: :Haematologica 2008
Ioana Borze Satu Mustjoki Eeva Juvonen Sakari Knuutila

| 1098 | haematologica | 2008; 93(7) lower than the wild-type, which is consistent with the low circulating levels of the abnormal chain (Figure 2B). These data demonstrate that this point mutation is associated to a severe reduction of the mutant mRNA expression level, which causes a β-thalassemia phenotype by eliciting β-globin chain deficiency. The molecular mechanisms responsible for impair...

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