نتایج جستجو برای: tuberous sclerosis complex tsc

تعداد نتایج: 845362  

Journal: :Cerebral cortex 2013
William W Lewis Mustafa Sahin Benoit Scherrer Jurriaan M Peters Ralph O Suarez Vanessa K Vogel-Farley Shafali S Jeste Matthew C Gregas Sanjay P Prabhu Charles A Nelson Simon K Warfield

The purpose of this study was to examine the relationship between language pathways and autism spectrum disorders (ASDs) in patients with tuberous sclerosis complex (TSC). An advanced diffusion-weighted magnetic resonance imaging (MRI) was performed on 42 patients with TSC and 42 age-matched controls. Using a validated automatic method, white matter language pathways were identified and microst...

Journal: :Genomics 1990
M Smith S Smalley R Cantor M Pandolfo M I Gomez R Baumann P Flodman K Yoshiyama Y Nakamura C Julier

Tuberous sclerosis (TSC) is a dominantly inherited disorder characterized by hamartomas and hamartias in one or more organs, most often in skin, brain, and kidneys. Analysis of the basic genetic defect in tuberous sclerosis would be greatly expedited by definitive determination of the chromosomal location of the TSC gene or genes. We have carried out genetic linkage studies in 15 TSC families, ...

2017
Okio Hino Toshiyuki Kobayashi

On July 10, 2016, Alfred G. Knudson, Jr., MD, PhD, a leader in cancer research, died at the age of 93 years. We deeply mourn his loss. Knudson's two-hit hypothesis, published in 1971, has been fundamental for understanding tumor suppressor genes and familial tumor-predisposing syndromes. To understand the molecular mechanism of two-hit-initiated tumorigenesis, Knudson used an animal model of a ...

Journal: :The Journal of clinical investigation 2017
Juxiang Cao Magdalena E Tyburczy Joel Moss Thomas N Darling Hans R Widlund David J Kwiatkowski

Tuberous sclerosis complex (TSC) is an autosomal dominant tumor-suppressor gene syndrome caused by inactivating mutations in either TSC1 or TSC2, and the TSC protein complex is an essential regulator of mTOR complex 1 (mTORC1). Patients with TSC develop hypomelanotic macules (white spots), but the molecular mechanisms underlying their formation are not fully characterized. Using human primary m...

Journal: :Journal of Immunology 2023

Abstract Tuberous sclerosis complex (TSC) is a multisystem disorder caused by loss-of-function mutations in TSC1/2 proteins. This results constitutive mTOR activation and predisposes to the development of benign tumours, with renal angiomyolipomas (AMLs) tuber-related drug-resistant epilepsy (DRE) being major causes morbidity mortality adults. Despite central role leukocyte biology beneficial i...

2014
John C Kingswood Paolo Bruzzi Paolo Curatolo Petrus J de Vries Carla Fladrowski Christoph Hertzberg Anna C Jansen Sergiusz Jozwiak Rima Nabbout Matthias Sauter Renaud Touraine Finbar O’Callaghan Bernard Zonnenberg Stefania Crippa Silvia Comis Guillaume Beaure d’Augères Elena Belousova Tom Carter Vincent Cottin Maria Dahlin José Carlos Ferreira Alfons Macaya Mirjana Perkovic Benedik Valentin Sander Sotirios Youroukos Ramon Castellana Bulent Ulker Martha Feucht

BACKGROUND Tuberous sclerosis complex (TSC) is a rare, multisystem, genetic disorder with an estimated prevalence between 1/6800 and 1/15000. Although recent years have seen huge progress in understanding the pathophysiology and in the management of TSC, several questions remain unanswered. A disease registry could be an effective tool to gain more insights into TSC and thus help in the develop...

Journal: :Neurobiology of disease 2012
Itzamarie Chévere-Torres Jordan M Maki Emanuela Santini Eric Klann

Tuberous sclerosis complex (TSC) is a genetic disorder characterized by the development of hamartomas in multiple organs. Neurological manifestation includes cortical dysplasia, epilepsy, and cognitive deficits such as mental impairment and autism. We measured the impact of TSC2-GAP mutations on cognitive processes and behavior in, ΔRG transgenic mice that express a dominant/negative TSC2 that ...

2014
Elena Lesma Silvia Ancona Silvia M Sirchia Emanuela Orpianesi Vera Grande Patrizia Colapietro Eloisa Chiaramonte Anna Maria Di Giulio Alfredo Gorio

Tuberous sclerosis complex (TSC) is caused by mutations in TSC1 or TSC2 genes. Lymphangioleiomyomatosis (LAM) can be sporadic or associated with TSC and is characterized by widespread pulmonary proliferation of abnormal α-smooth muscle (ASM)-like cells. We investigated the features of ASM cells isolated from chylous thorax of a patient affected by LAM associated with TSC, named LAM/TSC cells, b...

2017
Alvaro I. Ortiz Z. Pedro Luis Cárdenas Luis C. Escaf Marcela Peralta

Patients with retinal lesions related to tuberous sclerous complex (TSC) commonly have no impairment of visual acuity. We present a case of a 1-year-old Hispanic girl with TSC in which bilateral cortical blindness is documented.

Journal: :Behavior genetics 2011
Dan Ehninger Alcino J Silva

Tuberous sclerosis (TSC) is a single-gene disorder caused by heterozygous mutations in the TSC1 or TSC2 gene. TSC is often associated with neurological (e.g., epilepsy), cognitive (intellectual disabilities, specific neuropsychological impairments) and behavioral pathologies (e.g., autism, attention deficit hyperactivity disorder). In addition, there is a high prevalence of psychiatric problems...

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