نتایج جستجو برای: survival motor neuron gene

تعداد نتایج: 1595196  

Journal: :Neuron 2011
George Z. Mentis Dvir Blivis Wenfang Liu Estelle Drobac Melissa E. Crowder Lingling Kong Francisco J. Alvarez Charlotte J. Sumner Michael J. O'Donovan

To define alterations of neuronal connectivity that occur during motor neuron degeneration, we characterized the function and structure of spinal circuitry in spinal muscular atrophy (SMA) model mice. SMA motor neurons show reduced proprioceptive reflexes that correlate with decreased number and function of synapses on motor neuron somata and proximal dendrites. These abnormalities occur at an ...

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2007
Yaoming Wang Xiao Ou Mao Lin Xie Surita Banwait Hugo H Marti David A Greenberg Kunlin Jin

We sought genetic evidence for the involvement of neuronal vascular endothelial growth factor (VEGF) in amyotrophic lateral sclerosis (ALS). Mice expressing human ALS mutant superoxide dismutase-1 (SOD1) were crossed with mice that overexpress VEGF in neurons (VEGF+/+). We report that SOD1(G93A)/VEGF+/+ double-transgenic mice show delayed motor neuron loss, delayed motor impairment, and prolong...

Journal: :Archives of neurology 2009
William T Hu Harro Seelaar Keith A Josephs David S Knopman Bradley F Boeve Eric J Sorenson Leo McCluskey Lauren Elman Helenius J Schelhaas Joseph E Parisi Benno Kuesters Virginia M-Y Lee John Q Trojanowski Ronald C Petersen John C van Swieten Murray Grossman

BACKGROUND Frontotemporal dementia and amyotrophic lateral sclerosis are neurodegenerative diseases associated with TAR DNA-binding protein 43- and ubiquitin-immunoreactive pathologic lesions. OBJECTIVE To determine whether survival is influenced by symptom of onset in patients with frontotemporal dementia and amyotrophic lateral sclerosis. DESIGN, SETTING, AND PATIENTS Retrospective review...

Journal: :genetics in the 3rd millennium 0
صادق ولیان بروجنی sadeq valian brojeni molecular diagnosis section, isfahan medical genetics center, isfahan, iran. نیره نوری nayereh noori

defects in genes for survival motor neuron (smn) and neural apoptosis inhibitory proteins (naip) have been reported associated with spinal muscular atrophy (sma). among the genetic defects, deletions in exons 7 and 8 of smn and exons 4 and 5 of naip were found to be most significant. in the current study, 35 unrelated sma patients including 9 patients with type i, 6 with type ii, 20 with type i...

Journal: :Journal of neuropathology and experimental neurology 2012
Barry Gertz Margaret Wong Lee J Martin

Amyotrophic lateral sclerosis (ALS) is a fatal adult-onset neurodegenerative disease that causes degeneration of motor neurons and paralysis. Approximately 20% of familial ALS cases have been linked to mutations in the copper/zinc superoxide dismutase (SOD1) gene, but it is unclear how mutations in the protein result in motor neuron degeneration. Transgenic (tg) mice expressing mutated forms of...

Journal: :Frontiers in bioscience 2010
Thomas W Bebee Jordan T Gladman Dawn S Chandler

Proximal spinal muscular atrophy (SMA) is a neuromuscular disease caused by low levels of the survival motor neuron (SMN) protein. The reduced SMN levels are due to loss of the survival motor neuron-1 (SMN1) gene. Humans carry a nearly identical SMN2 gene that generates a truncated protein, due to a C to T nucleotide alteration in exon 7 that leads to inefficient RNA splicing of exon 7. This ex...

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