نتایج جستجو برای: smn1

تعداد نتایج: 481  

Journal: :Neurology 2006
C J Sumner S J Kolb G G Harmison N O Jeffries K Schadt R S Finkel G Dreyfuss K H Fischbeck

BACKGROUND Clinical trials of drugs that increase SMN protein levels in vitro are currently under way in patients with spinal muscular atrophy. OBJECTIVE To develop and validate measures of SMN mRNA and protein in peripheral blood and to establish baseline SMN levels in a cohort of controls, carriers, and patients of known genotype, which could be used to follow response to treatment. METHO...

2011
James N. Sleigh Thomas H. Gillingwater Kevin Talbot

Spinal muscular atrophy (SMA), which is caused by inactivating mutations in the survival motor neuron 1 (SMN1) gene, is characterized by loss of lower motor neurons in the spinal cord. The gene encoding SMN is very highly conserved in evolution, allowing the disease to be modeled in a range of species. The similarities in anatomy and physiology to the human neuromuscular system, coupled with th...

Journal: :Journal of neuromuscular diseases 2014
Duncan MacKenzie Fahad Shamim Kevin Mongeon Ankur Trivedi Alex MacKenzie Faraz Farooq

BACKGROUND Autosomal recessive spinal muscle atrophy (SMA) is characterized by the loss of α motor neurons resulting in progressive muscle loss and respiratory failure. SMA is one of the most common inherited causes of infant death with a carrier frequency of 1 in 50 and a calculated prevalence of about 1 in 11,000 live births in the US. The low amount of functional survival motor neuron (SMN) ...

Journal: :The Biochemical journal 2005
Raphaël Rouget François Vigneault Circé Codio Camille Rochette Isabelle Paradis Régen Drouin Louise R Simard

There exist two SMN (survival motor neuron) genes in humans, the result of a 500 kb duplication in chromosome 5q13. Deletions/mutations in the SMN1 gene are responsible for childhood spinal muscular atrophy, an autosomal recessive neurodegenerative disorder. While the SMN1 and SMN2 genes are not functionally equivalent, up-regulation of the SMN2 gene represents an important therapeutic target. ...

Journal: :American journal of medical genetics. Part A 2010
Thomas W Prior Pamela J Snyder Britton D Rink Dennis K Pearl Robert E Pyatt David C Mihal Todd Conlan Betsy Schmalz Laura Montgomery Katie Ziegler Carolee Noonan Sayaka Hashimoto Shannon Garner

Spinal muscular atrophy (SMA) is a common autosomal recessive neuromuscular disorder caused by mutations in the survival motor neuron (SMN1) gene, affecting approximately 1 in 10,000 live births. The homozygous absence of SMN1 exon 7 has been observed in the majority of patients and is being utilized as a reliable and sensitive SMA diagnostic test. Treatment and prevention of SMA are complement...

2017
Valérie Robin Graziella Griffith John-Paul L. Carter Christian J. Leumann Luis Garcia Aurélie Goyenvalle

Spinal muscular atrophy (SMA) is a recessive disease caused by mutations in the SMN1 gene, which encodes the protein survival motor neuron (SMN), whose absence dramatically affects the survival of motor neurons. In humans, the severity of the disease is lessened by the presence of a gene copy, SMN2. SMN2 differs from SMN1 by a C-to-T transition in exon 7, which modifies pre-mRNA splicing and pr...

Journal: :genetics in the 3rd millennium 0
امید آریانی omid ariani مرتضی بنیادی morteza bonyadi center of excellence for molecular analysis of smn gene biodiversity, department of genetics, faculty of natural sciences, university of tabriz, tabriz, iran محمد برزگر mohammad barzegar

spinal muscular atrophy (sma) is an autosomal recessive neuromuscular disorder characterized by degeneration of spinal cord anterior horn cells, leading to muscular atrophy. sma is clinically classified into three sub-groups based on the age of onset and severity. the majority of patients with sma have homozygous deletions of exons 7 and 8 of the survival motor neuron (smn) gene. the purpose of ...

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