نتایج جستجو برای: phenylketonuria pku

تعداد نتایج: 2694  

2016
Vibeke M. Bruinenberg Danique van Vliet Amos Attali Martijn C. de Wilde Mirjam Kuhn Francjan J. van Spronsen Eddy A. van der Zee

The inherited metabolic disease phenylketonuria (PKU) is characterized by increased concentrations of phenylalanine in the blood and brain, and as a consequence neurotransmitter metabolism, white matter, and synapse functioning are affected. A specific nutrient combination (SNC) has been shown to improve synapse formation, morphology and function. This could become an interesting new nutritiona...

Journal: :Molecular Genetics and Metabolism Reports 2018

Journal: :Clinical chemistry 1997
S T Wang S Pizzolato H P Demshar

We used ROC plots to evaluate the clinical performance of the Guthrie, Wallac, and Isolab assays for newborn phenylketonuria (PKU) screening and assessed the screening discriminatory power of these three assays by the area under the ROC plot, Youden's J index, and the likelihood ratio. The use of these plots not only allows us to pinpoint the exact cutoff value in screening, but also provides a...

Journal: :Pediatrics 2003
Harald E Möller Josef Weglage Ulrich Bick Dirk Wiedermann Reinhold Feldmann Kurt Ullrich

Magnetic resonance imaging studies in patients with phenylketonuria (PKU) revealed white matter alterations that correlated to most recent blood phenylalanine (Phe) concentrations as well as to brain Phe concentrations measured by magnetic resonance spectroscopy. The clinical significance of these changes is unknown. Magnetic resonance imaging data thus have no impact on therapeutic recommendat...

Journal: :Journal of medical genetics 1998
I Rivera P Leandro U Lichter-Konecki I Tavares de Almeida M C Lechner

In order to elucidate the molecular basis of phenylketonuria (PKU) in Portugal, a detailed study of the Portuguese mutant phenylalanine hydroxylase (PAH) genes was performed. A total of 222 mutant alleles from 111 PKU families were analysed for 26 mutations and restriction fragment length polymorphismlvariable number tandem repeat (RFLP/VNTR) haplotypes. It was possible to characterise 55% of t...

Journal: :Nature Communications 2021

Abstract Phenylketonuria (PKU) is caused by autosomal recessive variants in phenylalanine hydroxylase ( PAH ), leading to systemic accumulation of L-phenylalanine (L-Phe) that may reach neurotoxic levels. A homozygous Pah - R261Q mouse, with a highly prevalent misfolding variant humans, reveals the expected hepatic activity decrease, L-Phe increase, L-tyrosine and L-tryptophan tetrahydrobiopter...

2016
Anita MacDonald T. Alexander Smith Shamika de Silva Veronica Alam Jeanni M.T. van Loon

INTRODUCTION Management of phenylketonuria (PKU) is mainly achieved through strict dietary control that aims to limit the intake of phenylalanine (Phe). Adherence to this diet is burdensome due to the need for specially prepared low-Phe meals and regular monitoring of Phe concentrations. A UK cross-sectional study was conducted to identify the personal time and monetary burden associated with a...

2013
Heather Donald Morag C. E. McFadyen Susanne P. Boyle

This new initiative across the School of Pharmacy and Life Sciences at Robert Gordon University focuses around students from the Overseas Pharmacist’s Assessment Programme (OSPAP) and 3rd year Nutrition and Dietetics students working in an interprofessional setting to manage the care of individuals with Phenylketonuria (PKU). A problem based learning approach was employed which involved small g...

Journal: :Molecular genetics and metabolism 2012
Amy Cunningham Heather Bausell Mary Brown Maggie Chapman Kari DeFouw Sharon Ernst Julie McClure Helen McCune Donna O'Steen Amy Pender Jill Skrabal Ann Wessel Elaina Jurecki Renée Shediac Suyash Prasad Jane Gillis Stephen Cederbaum

Phenylketonuria (PKU) is an inherited disorder of phenylalanine (Phe) metabolism. Until recently, the only treatment for PKU was a Phe-restricted diet. Increasing evidence of suboptimal outcomes in diet-treated individuals, inconsistent PKU management practices, and the recent availability of tetrahydrobiopterin (BH(4)) therapy have fueled the need for new management and treatment recommendatio...

2017
E. Vieira H.S. Maia C.B. Monteiro L.M. Carvalho T. Tonon A.P. Vanz I.V.D. Schwartz M.G. Ribeiro

Early dietary treatment of phenylketonuria (PKU), an inborn error of phenylalanine (Phe) metabolism, results in normal cognitive development. Although health-related quality of life (HRQoL) of PKU patients has been reported as unaffected in high-income countries, there are scarce data concerning HRQoL and adherence to treatment of PKU children and adolescents from Brazil. The present study comp...

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