نتایج جستجو برای: missense

تعداد نتایج: 12396  

Journal: :Atherosclerosis 2010
C Candini A W Schimmel J Peter A E Bochem A G Holleboom M Vergeer R P F Dullaart G M Dallinga-Thie G K Hovingh K L Khoo T Fasano L Bocchi S Calandra J A Kuivenhoven M M Motazacker

OBJECTIVES The current literature provides little information on the frequency of mutations in the ATP-binding cassette transporter A1 (ABCA1) in patients with low high-density lipoprotein cholesterol (HDL) levels that are referred to the clinic. In 78 patients with low plasma levels of HDL cholesterol that were referred to our clinic, we routinely screened for ABCA1 gene mutations and studied ...

2016
Alexander J. Cole Trisha Dwight Anthony J. Gill Kristie-Ann Dickson Ying Zhu Adele Clarkson Gregory B. Gard Jayne Maidens Susan Valmadre Roderick Clifton-Bligh Deborah J. Marsh

The tumour suppressor p53 is mutated in cancer, including over 96% of high-grade serous ovarian cancer (HGSOC). Mutations cause loss of wild-type p53 function due to either gain of abnormal function of mutant p53 (mutp53), or absent to low mutp53. Massively parallel sequencing (MPS) enables increased accuracy of detection of somatic variants in heterogeneous tumours. We used MPS and immunohisto...

Journal: :American journal of human genetics 2018
Magdalena Koczkowska Yunjia Chen Tom Callens Alicia Gomes Angela Sharp Sherrell Johnson Meng-Chang Hsiao Zhenbin Chen Meena Balasubramanian Christopher P Barnett Troy A Becker Shay Ben-Shachar Debora R Bertola Jaishri O Blakeley Emma M M Burkitt-Wright Alison Callaway Melissa Crenshaw Karin S Cunha Mitch Cunningham Maria D D'Agostino Karin Dahan Alessandro De Luca Anne Destrée Radhika Dhamija Marica Eoli D Gareth R Evans Patricia Galvin-Parton Jaya K George-Abraham Karen W Gripp Jose Guevara-Campos Neil A Hanchard Concepcion Hernández-Chico LaDonna Immken Sandra Janssens Kristi J Jones Beth A Keena Aaina Kochhar Jan Liebelt Arelis Martir-Negron Maurice J Mahoney Isabelle Maystadt Carey McDougall Meriel McEntagart Nancy Mendelsohn David T Miller Geert Mortier Jenny Morton John Pappas Scott R Plotkin Dinel Pond Kenneth Rosenbaum Karol Rubin Laura Russell Lane S Rutledge Veronica Saletti Rhonda Schonberg Allison Schreiber Meredith Seidel Elizabeth Siqveland David W Stockton Eva Trevisson Nicole J Ullrich Meena Upadhyaya Rick van Minkelen Helene Verhelst Margaret R Wallace Yoon-Sim Yap Elaine Zackai Jonathan Zonana Vickie Zurcher Kathleen Claes Yolanda Martin Bruce R Korf Eric Legius Ludwine M Messiaen

Neurofibromatosis type 1 (NF1), a common genetic disorder with a birth incidence of 1:2,000-3,000, is characterized by a highly variable clinical presentation. To date, only two clinically relevant intragenic genotype-phenotype correlations have been reported for NF1 missense mutations affecting p.Arg1809 and a single amino acid deletion p.Met922del. Both variants predispose to a distinct mild ...

Journal: :Human molecular genetics 2005
Fred B Berry Yahya Tamimi Michelle V Carle Ordan J Lehmann Michael A Walter

The FOX family of transcription factor genes is an evolutionary conserved, yet functionally diverse class of transcription factors that are important for regulation of energy homeostasis, development and oncogenesis. The proteins encoded by FOX genes are characterized by a conserved DNA-binding domain known as the forkhead domain (FHD). To date, disease-causing mutations have been identified in...

Journal: :Journal of thrombosis and haemostasis : JTH 2011
K Ogata S R Selvaraj H Z Miao S W Pipe

UNLABELLED BACKGROUND & OBJECTIVE  The factor VIII (FVIII) B domain shares very little amino acid homology with other known proteins and is not directly necessary for procoagulant activity. Despite this, missense mutations within the B domain have been reported in patients with hemophilia A. Given that the B domain is dispensable for secretion and function of FVIII, we hypothesized that thes...

2016
Ji-Yeon Kim Kyunghee Park Hae Hyun Jung Eunjin Lee Eun Yoon Cho Kwang Hee Lee Soo Youn Bae Se Kyung Lee Seok Won Kim Jeong Eon Lee Seok Jin Nam Jin Seok Ahn Young-Hyuck Im Yeon Hee Park

PURPOSE TP53, the most frequently mutated gene in breast cancer, is more frequently altered in HER2-enriched and basal-like breast cancer. However, no studies have clarified the role of TP53 status as a prognostic and predictive marker of triple-negative breast cancer (TNBC). MATERIALS AND METHODS We performed p53 immunohistochemistry (IHC), nCounter mRNA expression assay, and DNA sequencing ...

Journal: :Clinical genetics 2012
D O Robinson F Lin M Lyon M Raponi E Cross H E White H Cox J Clayton-Smith D Baralle

Defects at the level of pre-mRNA splicing are a common source of genetic mutation but such mutations are not always easy to identify from DNA sequence data alone. Clinical practice has only recently begun to incorporate analysis for this type of abnormality. Some base changes at the DNA level currently viewed as unclassified variants or missense mutations may influence RNA splicing. To address ...

2017
Wei Wei Chunlei Zheng Min Zhu Xiaofan Zhu Renchi Yang Saurav Misra Bin Zhang

Missense mutation is the most common mutation type in hemophilia. However, the majority of missense mutations remain uncharacterized. Here we characterize how hemophilia mutations near the unused N-glycosylation site of the A2 domain (N582) of FVIII affect protein conformation and intracellular trafficking. N582 is located in the middle of a short 310-helical turn (D580-S584), in which most ami...

2013
Sandra Deliard Saarene Panossian Frank D. Mentch Cecilia E. Kim Cuiping Hou Edward C. Frackelton Jonathan P. Bradfield Joseph T. Glessner Haitao Zhang Kai Wang Patrick M.A. Sleiman Rosetta M. Chiavacci Robert I. Berkowitz Hakon Hakonarson Jianhua Zhao Struan F.A. Grant

OBJECTIVE Common variation at the loci harboring fat mass and obesity (FTO), melanocortin receptor 4 (MC4R), and transmembrane protein 18 (TMEM18) is consistently reported as being statistically most strongly associated with obesity. Investigations if these loci also harbor rarer missense variants that confer substantially higher risk of common childhood obesity in African American (AA) childre...

Journal: :Haematologica 2007
Michal Zucker Ariella Zivelin Meytal Landau Ophira Salomon Gili Kenet Frederic Bauduer Michel Samama Jacqueline Conard Marie-Hélène Denninger Abu-Samra Hani Micheline Berruyer Donald Feinstein Uri Seligsohn

BACKGROUND AND OBJECTIVES Factor XI (FXI) deficiency is a rare autosomal recessive disorder, the main manifestation of which is injury-related bleeding. The disorder is rare in most populations, but common among Jews in whom two mutations, E117X and F283L, account for 98% of cases. Other mutations, C38R and C128X, are prevalent in French Basques and Britons, respectively. Additional sporadic mu...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید