نتایج جستجو برای: linked lymphoproliferative syndrome

تعداد نتایج: 843487  

Journal: :Journal of immunology 1999
S G Tangye S Lazetic E Woollatt G R Sutherland L L Lanier J H Phillips

The genetic defect in X-linked lymphoproliferative syndrome (XLP) is the Src homology 2 domain-containing protein SAP. SAP constitutively associates with the cell surface molecule, signaling lymphocytic activation molecule (SLAM), and competes with SH2-domain containing protein tyrosine phosphatase-2 (SHP-2) for recruitment to SLAM. SLAM exhibits homology with the mouse cell surface receptor 2B...

Journal: :Pediatrics 2013
Amanda Rudman Spergel Kelly Walkovich Susan Price Julie E Niemela Dowain Wright Thomas A Fleisher V Koneti Rao

Autoimmune lymphoproliferative syndrome (ALPS) is a rare inherited disorder of apoptosis, most commonly due to mutations in the FAS (TNFRSF6) gene. It presents with chronic lymphadenopathy, splenomegaly, and symptomatic multilineage cytopenias in an otherwise healthy child. Unfortunately, these clinical findings are also noted in other childhood lymphoproliferative conditions, such as leukemia,...

Journal: :Pediatrics 2012
Ester Mejstríková Ales Janda Ondrej Hrusák Hana Bucková Markéta Vlcková Miroslava Hancárová Tomás Freiberger Barbora Ravcuková Karel Vesely Lenka Fajkusová Lenka Kopecková David Sumerauer Edita Kabícková Anna Sedivá Jan Stary Zdenek Sedlácek

SH2D1A gene defects are the cause of X-linked lymphoproliferative disorder (XLP-1), a rare condition characterized by severe immune dysregulation. We present a patient lacking the typical symptoms of XLP-1, but experiencing a severe unusual skin condition encompassing features of dermatosclerosis and vesiculobullous skin disease. A maternal cousin of the patient was diagnosed with XLP-1 and fou...

Aflatoonian Mahin Badakhsh Hoda Fadai Fahameh Farajzadeh Saeedeh Khalili Maryam Mohammadi Saman Mohebbi Azadeh

Goltz syndrome or focal dermal hypoplasia is a rare syndrome with mesoectodermal hypoplasia. This syndrome is an X-linked dominant disorder with involvement of the cutaneous, ocular, dental and skeletal systems. The most significant feature of this disease is connective tissue dysplasia. Here, we report a 30-year old woman who presented with congenital unilateral linear atrophic areas on her tr...

Journal: :iranian journal of medical sciences 0
mitra basiratnia shiraz nephrology-urology research center, shiraz university of medical sciences, shiraz, iran alireza baradaran-heravi child and family research institute, department of medical genetics, university of british columbia, vancouver, canada majid yavarian hematology research center, shiraz university of medical sciences, shiraz, iran bita geramizadeh department of pathology, shiraz university of medical sciences, shiraz, iran mehran karimi hematology research center, shiraz university of medical sciences, shiraz, iran

schimke immuno-osseous dysplasia is a rare autosomal recessive multisystem disorder characterized by steroid-resistant nephrotic syndrome, immunodeficiency, and spondyloepiphy-seal dysplasia. mutations in swi/snf2 related, matrix associated, actin dependent regulator of chromatin, subfamily a-like 1 (smarcal1) gene are responsible for the disease. the present report describes, for the first tim...

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