نتایج جستجو برای: spinocerebellar ataxia type 1 gene

تعداد نتایج: 4353782  

2015
K. Sato K. Ishigame S.H. Ying K. Oishi M.I. Miller S. Mori

BACKGROUND AND PURPOSE Site-specific degeneration patterns of the infratentorial brain in relation to phylogenetic origins may relate to symptoms in patients with spinocerebellar degeneration, but the patterns are still unclear. We investigated macro- and microstructural changes of the infratentorial brain based on phylogenetic origins and their correlation with symptoms in patients with spinoc...

2014
Genko Oyama Amanda Thompson Kelly D. Foote Natlada Limotai Muhammad Abd-El-Barr Nicholas Maling Irene A. Malaty Ramon L. Rodriguez Sankarasubramoney H. Subramony Testuo Ashizawa Michael S. Okun

BACKGROUND Deep brain stimulation (DBS) has been utilized to treat various symptoms in patients suffering from movement disorders such as Parkinson's disease, dystonia, and essential tremor. Though ataxia syndromes have not been formally or frequently addressed with DBS, there are patients with ataxia and associated medication refractory tremor or dystonia who may potentially benefit from thera...

2013
Paola Michieletto Andrea Martinuzzi Stefano Pensiero

Purpose: To disclose the association between spinocerebellar ataxia with oculomotor apraxia and high grade (7 diopters) congenital astigmatism. Methods: Single observational case report. A 39-year-old patient affected by spinocerebellar ataxia from the age of 20 was submitted to genetic and ophthalmic investigations to reach a diagnosis. Results: Genetic testing did not lead to a sure diagnosis...

2016
Amy Moriarty Arron Cook Helen Hunt Matthew E. Adams Lisa Cipolotti Paola Giunti

BACKGROUND The natural history of clinical symptoms in the spinocerebellar ataxias (SCA)s has been well characterised. However there is little longitudinal data comparing cognitive changes in the most common SCA subtypes over time. The present study provides a preliminary longitudinal characterisation of the clinical and cognitive profiles in patients with SCA1, SCA2, SCA3, SCA6 and SCA7, with ...

Journal: :Movement disorders : official journal of the Movement Disorder Society 2013
Anna Molloy Okka Kimmich Joanne Martindale Helena Moore Michael Hutchinson Sean O'Riordan

CACNA1A mutations cause a range of disorders with diverse, sometimes overlapping clinical features. Point mutations, including missense mutations, nonsense mutations, splicing mutations and small deletions/insertions, result in a variety of phenotypes including episodic ataxia type 2 (EA2) and familial hemiplegic migraine type 1 (FHM1). These 2 conditions show clinical overlap with spinocerebel...

Journal: :Brain : a journal of neurology 2014
Jérôme Delplanque David Devos Vincent Huin Alexandre Genet Olivier Sand Caroline Moreau Cyril Goizet Perrine Charles Mathieu Anheim Marie Lorraine Monin Luc Buée Alain Destée Guillaume Grolez Christine Delmaire Kathy Dujardin Delphine Dellacherie Alexis Brice Giovanni Stevanin Isabelle Strubi-Vuillaume Alexandra Dürr Bernard Sablonnière

Autosomal dominant cerebellar ataxia corresponds to a clinically and genetically heterogeneous group of neurodegenerative disorders that primarily affect the cerebellum. Here, we report the identification of the causative gene in spinocerebellar ataxia 21, an autosomal-dominant disorder previously mapped to chromosome 7p21.3-p15.1. This ataxia was firstly characterized in a large French family ...

2017
Cheng-Tsung Hsiao Yo-Tsen Liu Yi-Chu Liao Ting-Yi Hsu Yi-Chung Lee Bing-Wen Soong

BACKGROUND The inositol 1,4,5-triphosphate (IP3) receptor type 1 gene (ITPR1) encodes the IP3 receptor type 1 (IP3R1), which modulates intracellular calcium homeostasis and signaling. Mutations in ITPR1 have been implicated in inherited cerebellar ataxias. The aim of this study was to investigate the role of ITPR1 mutations, including both large segmental deletion and single nucleotide mutation...

Journal: :Neurobiology of aging 2013
Xiaolu Liu Ming Lu Lu Tang Nan Zhang Dehua Chui Dongsheng Fan

Amyotrophic lateral sclerosis (ALS) is a fatal neurodegenerative disorder with unclear etiology. Recently, intermediate CAG repeat expansions in ATXN2, the gene responsible for spinocerebellar ataxia type 2 (SCA2), have been identified as a possible genetic risk factor for ALS. In this study, we analyzed the ATXN2 CAG repeat length in Chinese patients with ALS to evaluate the relationship betwe...

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