نتایج جستجو برای: lebers congenital amaurosis

تعداد نتایج: 120868  

Journal: :Stroke 1975
D H Slepyan R M Rankin C Stahler G E Gibbons

Amaurosis fugax (transient monocular blindness) is a symptom of retinal ischemia just as contralateral hemiparesis and sensory loss are symptoms of cerebral ischemia. These symptoms are produced by atherosclerotic stenosis of the carotid vessels at the ipsilateral carotid bifurcation and emboli from these areas causing focal, repetitive, retinal ischemia. A study of 31 endarterectomy patients w...

Journal: :Human molecular genetics 2009
Mei Hong Tan Alexander J Smith Basil Pawlyk Xiaoyun Xu Xiaoqing Liu James B Bainbridge Mark Basche Jenny McIntosh Hoai Viet Tran Amit Nathwani Tiansen Li Robin R Ali

Defects in the photoreceptor-specific gene encoding aryl hydrocarbon receptor-interacting protein-like 1 (AIPL1) are clinically heterogeneous and present as Leber Congenital Amaurosis, the severest form of early-onset retinal dystrophy and milder forms of retinal dystrophies such as juvenile retinitis pigmentosa and dominant cone-rod dystrophy. [Perrault, I., Rozet, J.M., Gerber, S., Ghazi, I.,...

Journal: :PLoS Medicine 2006
Alexis-Pierre Bemelmans Corinne Kostic Sylvain V Crippa William W Hauswirth Janis Lem Francis L Munier Mathias W Seeliger Andreas Wenzel Yvan Arsenijevic

BACKGROUND RPE65 is specifically expressed in the retinal pigment epithelium and is essential for the recycling of 11-cis-retinal, the chromophore of rod and cone opsins. In humans, mutations in RPE65 lead to Leber congenital amaurosis or early-onset retinal dystrophy, a severe form of retinitis pigmentosa. The proof of feasibility of gene therapy for RPE65 deficiency has already been establish...

Journal: :Advances in experimental medicine and biology 2006
Sylvain Hanein Isabelle Perrault Sylvie Gerber Hélène Dollfus Jean-Louis Dufier Josué Feingold Arnold Munnich Shomi Bhattacharya Josseline Kaplan José-Alain Sahel Jean-Michel Rozet Thierry Leveillard

Leber congenital amaurosis (LCA) is the most early and severe form of all inherited retinal dystrophies, responsible for congenital blindness. The genetic heterogeneity of LCA has been accepted for a long time but it turned out to be largely higher than all odds. So far, 11genes have been mapped on human chromosomes and eight identified. i) the retinal specific guanylate cyclase gene (GUCY2D, r...

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