نتایج جستجو برای: ichthyosis linearis circumflexa

تعداد نتایج: 2339  

Journal: :Indian Dermatology Online Journal 2013

Journal: :Proceedings of the Royal Society of Medicine 1915

2009
Farid Rezaei Moghaddam Farid Safar Mahsa Asheghan Zahra Reza Soltani Fatemeh Dehghani Zade

Sjögren-Larsson syndrome is a rare autosomal recessive disorder that was originally recognized in the coexistence of congenital ichthyosis, spastic diplegia or quadriplegia and mental retardation. We recently saw two cases with characteristic features of this rare syndrome. Two brothers aged 21 and 25 years presented with triad of congenital ichthyosis, mental retardation and spastic diplegia. ...

Journal: :Pediatric dermatology 2014
Clare Kiely Deirdre Devaney Judith Fischer Patricia Lenane Alan D Irvine

Ichthyosis prematurity syndrome (IPS; Mendelian Inheritance in Man 608649) is classified as a syndromic autosomal recessive ichthyosis. Here we describe two siblings with IPS and report a recurrent homozygous mutation (c.1430T>A) that is predicted to lead to a p.Val477Asp substitution in fatty acid transport protein 4. This mutation has arisen for the second time in an entirely distinct populat...

2015
Hayley Leight Zachary Zinn Omid Jalali

Here, we report a case of a middle-aged woman presenting with severe, long-standing, hyperkeratotic plaques of the lower extremities unrelieved by over-the-counter medications. Initial history and clinical findings were suggestive of an inherited ichthyosis. Ichthyoses are genetic disorders characterized by dry scaly skin and altered skin-barrier function. A diagnosis of ichthyosis vulgaris was...

Journal: :Annals of tropical paediatrics 2011
G Rossi D Mesia

Harlequin ichthyosis (HI) is a very rare severe form of autosomal recessive congenital ichthyosis, usually associated with stillbirth and early neonatal death. A newborn girl with HI is described. She presented in a critical condition with severe universalis hyperkeratosis, diffuse scales and deep erythematous fissures. She received preventive systemic antibiotics and hygienic nursing with skin...

2014
Isabelle Dreyfus Cécile Chouquet Khaled Ezzedine Sophie Henner Christine Chiavérini Aude Maza Sandrine Pascal Lauriane Rodriguez Pierre Vabres Ludovic Martin Stéphanie Mallet Sébastien Barbarot Jérôme Dupuis Juliette Mazereeuw-Hautier

BACKGROUND Inherited ichthyoses represent a group of rare skin disorders characterized by scaling, hyperkeratosis and inconstant erythema, involving most of the tegument. Epidemiology remains poorly described. This study aims to evaluate the prevalence of inherited ichthyosis (excluding very mild forms) and its different clinical forms in France. METHODS Capture - recapture method was used fo...

Journal: :Child neurology open 2017
Tina Hsu Carrie C Coughlin Kristin G Monaghan Elise Fiala Robert C McKinstry Alex R Paciorkowski Marwan Shinawi

Synaptosomal-associated protein 29 (SNAP29) is a t-SNARE protein that is implicated in intracellular vesicle fusion. Mutations in the SNAP29 gene have been associated with cerebral dysgenesis, neuropathy, ichthyosis, and keratoderma syndrome (CEDNIK). In patients with 22q11.2 deletion syndrome, mutations in SNAP29 on the nondeleted chromosome are linked to similar ichthyotic and neurological ph...

Journal: :Diagnostic Pathology 2006
Oluwole Fadare

Ichthyosis uteri is an exceedingly rare condition in which the entire surface of the endometrium is replaced by stratified squamous epithelium. Originally described as an endometrial response to iatrogenically-introduced caustic substances, similar changes have since been described in association with a variety of inflammatory conditions of the endometrium. We describe herein a heretofore undes...

Journal: :Archives of Dermatology 2011

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