نتایج جستجو برای: bethlem myopathy

تعداد نتایج: 12325  

2012
ANTONELLA TAGLIA PAOLA D'AMBROSIO ALBERTO PALLADINO LUISA POLITANO

Nemaline myopathy is a rare congenital disease that generally occurs in childhood. We report a case of a 50-year-old man who presented with severe heart failure as the initial manifestation of nemaline myopathy. Soon after he developed acute restrictive respiratory failure due to the diaphragmatic paralysis. The diagnosis of "nemaline myopathy" was obtained on muscle biopsy performed one year l...

2015
Alessandra Ruggieri Francesco Brancati Simona Zanotti Lorenzo Maggi Maria Barbara Pasanisi Simona Saredi Chiara Terracciano Carlo Antozzi Maria Rosaria D′Apice Federica Sangiuolo Giuseppe Novelli Christian R. Marshall Stephen W. Scherer Lucia Morandi Luca Federici Roberto Massa Marina Mora Berge A. Minassian

INTRODUCTION Protein aggregation is a common cause of neuropathology. The protein aggregation myopathy Limb-Girdle Muscular Dystrophy 1D (LGMD1D) is caused by mutations of amino acids Phe89 or Phe93 of DNAJB6, a co-chaperone of the HSP70 anti-aggregation protein. Another DNAJB6 mutation, Pro96Arg, was found to cause a distal-onset myopathy in one family. RESULTS We detail the mutational, neur...

2017
Li-Yuan Sun Xiao-Ling Chu

RATIONALE We report a case of acute steroid myopathy in a patient with eczema receiving one dose of intra-muscular injection of Compound betamethasone. PATIENT CONCERNS Acute steroid myopathy (ASM) is usually caused by exogenous corticosteroids, and typically, occurs with therapy using intravenous corticosteroids at high doses. DIAGNOSES The patient was considered as a diagnosis of acute st...

2014
Chunkui Zhou Limin Wu Fengming Ni Wei Ji Jiang Wu Hongliang Zhang

Critical illness polyneuropathy and critical illness myopathy are frequent complications of severe illness that involve sensorimotor axons and skeletal muscles, respectively. Clinically, they manifest as limb and respiratory muscle weakness. Critical illness polyneuropathy/myopathy in isolation or combination increases intensive care unit morbidity via the inability or difficulty in weaning the...

Journal: :American journal of human genetics 2004
Christopher Meredith Ralf Herrmann Cheryl Parry Khema Liyanage Danielle E Dye Hayley J Durling Rachael M Duff Kaye Beckman Marianne de Visser Maaike M van der Graaff Peter Hedera John K Fink Elizabeth M Petty Phillipa Lamont Vicki Fabian Leslie Bridges Thomas Voit Frank L Mastaglia Nigel G Laing

We previously linked Laing-type early-onset autosomal dominant distal myopathy (MPD1) to a 22-cM region of chromosome 14. One candidate gene in the region, MYH7, which is mutated in cardiomyopathy and myosin storage myopathy, codes for the myosin heavy chain of type I skeletal muscle fibers and cardiac ventricles. We have identified five novel heterozygous mutations--Arg1500Pro, Lys1617del, Ala...

Journal: :The Canadian journal of neurological sciences. Le journal canadien des sciences neurologiques 1998
D Zochodne

Myopathies that occur in the intensive care unit can be divided into preexisting myopathies or newly acquired myopathies that develop in the intensive care unit. Myotonic dystrophy is an example of a preexisting myopathy that may render patients susceptible to acute respiratory failure following surgical procedures and anaesthesia. A group of myopathies that develop within the intensive care un...

Journal: :Journal of applied physiology 2009
Tina Wenz Francisca Diaz Dayami Hernandez Carlos T Moraes

Defects in the mitochondrial ATP-generating system are one of the most commonly inherited neurological disorders, but they remain without treatment. We have recently shown that modulation of the peroxisome proliferator-activated receptor-gamma coactivator-1alpha (PGC-1alpha) level in skeletal muscle of a mitochondrial myopathy mouse model offers a therapeutic approach. Here we analyzed if endur...

Journal: :The New England journal of medicine 2008
E Link S Parish J Armitage L Bowman S Heath F Matsuda I Gut M Lathrop R Collins

BACKGROUND Lowering low-density lipoprotein cholesterol with statin therapy results in substantial reductions in cardiovascular events, and larger reductions in cholesterol may produce larger benefits. In rare cases, myopathy occurs in association with statin therapy, especially when the statins are administered at higher doses and with certain other medications. METHODS We carried out a geno...

Journal: :American heart journal 2010
Soko Setoguchi John M Higgins Helen Mogun Vamsi K Mootha Jerry Avorn

BACKGROUND A recent large-scale, chemical screening study raised the hypothesis that propranolol may increase the risk of myopathy. We tested this hypothesis in a large population to assess whether (1) propranolol use is associated with an increased risk of myopathy and (2) the concurrent use of propranolol with a statin may further increase risk of myopathy. METHODS New users of propranolol ...

Journal: :Proceedings of the Royal Society of Medicine 1913

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