نتایج جستجو برای: macrocephaly

تعداد نتایج: 695  

Journal: :Journal of medical genetics 2001
R Bayoumi K Saar Y A Lee G Nürnberg A Reis M Nur-E-Kamal L I Al-Gazali

BACKGROUND We have previously described an autosomal recessive syndrome of macrocephaly, multiple epiphyseal dysplasia (MED), and distinctive facies in a large, extended Omani family. The MED observed seems to be part of a larger malformation syndrome, since both craniofacial and central nervous system changes were present in the family. We performed a whole genome scan in this family in order ...

Journal: :Clinical genetics 2013
A Gammon K Jasperson R Pilarski Tw Prior S Kuwada

We present the first known case of somatic PTEN mosaicism causing features of Cowden syndrome (CS) and inheritance in the subsequent generation. A 20-year-old woman presented for genetics evaluation with multiple ganglioneuromas of the colon. On examination, she was found to have a thyroid goiter, macrocephaly, and tongue papules, all suggestive of CS. However, her reported family history was n...

2016
Rikke S. Møller Sarah Weckhuysen Mathilde Chipaux Elise Marsan Valerie Taly E. Martina Bebin Susan M. Hiatt Jeremy W. Prokop Kevin M. Bowling Davide Mei Valerio Conti Pierre de la Grange Sarah Ferrand-Sorbets Georg Dorfmüller Virginie Lambrecq Line H.G. Larsen Eric Leguern Renzo Guerrini Guido Rubboli Gregory M. Cooper Stéphanie Baulac

OBJECTIVE To assess the prevalence of somatic MTOR mutations in focal cortical dysplasia (FCD) and of germline MTOR mutations in a broad range of epilepsies. METHODS We collected 20 blood-brain paired samples from patients with FCD and searched for somatic variants using deep-targeted gene panel sequencing. Germline mutations in MTOR were assessed in a French research cohort of 93 probands wi...

Journal: :Journal of Clinical Neuroscience 2016

Journal: :Journal of medical genetics 1997
K H Orstavik P Strømme J Ek A Torvik O H Skjeldal

We report two sisters with macrocephaly, epilepsy, and severe mental retardation. The first child was a 14 year old girl born at term after a normal pregnancy, with birth weight 3600 g and occipitofrontal circumference (OFC) 36 cm (75th centile). Her head size increased markedly during the first six months of life, and was later stable at 2-3 cm above the 97.5th centile. Her development was cha...

Journal: :Neurobiology of disease 2006
Luis Federico Bátiz Patricia Páez Antonio J Jiménez Sara Rodríguez Carolina Wagner José Manuel Pérez-Fígares Esteban Martín Rodríguez

The hyh mouse carrying a point mutation in the gene encoding for soluble N-ethylmaleimide-sensitive factor (NSF) attachment protein alpha (alpha-SNAP) develops inherited hydrocephalus. The investigation was designed to study: (i) the clinical evolution of hyh mice; (ii) factors other than the alpha-SNAP mutation that may influence the expression of hydrocephalus; (iii) the neuropathological fea...

2017
Zahra PIRZADEH Massoud HOUSHMAND Jafar NASIRI Mohsen MOLLAMOHAMMADI Mostafa SEDIGHI Seyed Hassan TONEKABONI

Objective Glutaricaciduria type 1 (GA1), is a rare, treatable neuro metabolic disease, due to glutaryl- CoA dehydrogenase (GCDH) gene mutation.In regions without neonatal blood screening (NBS), patients are diagnosed in symptomatic period. This study was carried out to assess patients with GA1 for clinical, biochemical, neuroimaging findings and GCDH gene mutations analysis. Materials & Metho...

2004
Johan Ek Ansgar Torvik Ola H Skjeldal

We report two sisters with macrocephaly, epilepsy, and severe mental retardation. The first child was a 14 year old girl born at term after a normal pregnancy, with birth weight 3600 g and occipitofrontal circumference (OFC) 36 cm (75th centile). Her head size increased markedly during the first six months of life, and was later stable at 2-3 cm above the 97.5th centile. Her development was cha...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید