نتایج جستجو برای: scn1a mutations

تعداد نتایج: 173129  

Journal: :Iranian journal of basic medical sciences 2015
Soha Namazi Negar Azarpira Katayoon Javidnia Mehrdad Emami Rahimeh Rahjoo Razieh Berahmand Afshin Borhani-Haghighi

OBJECTIVE S From a genetic point of view, epilepsy is a polygenic multifactorial syndrome. The SCN1A and B genes belong to a family of genes that provide instructions for making sodium channels. Understanding the relevance of SCN1A and SCN1B gene polymorphisms to plasma concentration of carbamazepine (CBZ) and 'its active metabolite carbamazepine 10, 11 epoxide (CBZE), may shed more light on in...

Journal: :Human molecular genetics 2012
Michael Steffens Costin Leu Ann-Kathrin Ruppert Federico Zara Pasquale Striano Angela Robbiano Giuseppe Capovilla Paolo Tinuper Antonio Gambardella Amedeo Bianchi Angela La Neve Giovanni Crichiutti Carolien G F de Kovel Dorothée Kasteleijn-Nolst Trenité Gerrit-Jan de Haan Dick Lindhout Verena Gaus Bettina Schmitz Dieter Janz Yvonne G Weber Felicitas Becker Holger Lerche Bernhard J Steinhoff Ailing A Kleefuß-Lie Wolfram S Kunz Rainer Surges Christian E Elger Hiltrud Muhle Sarah von Spiczak Philipp Ostertag Ingo Helbig Ulrich Stephani Rikke S Møller Helle Hjalgrim Leanne M Dibbens Susannah Bellows Karen Oliver Saul Mullen Ingrid E Scheffer Samuel F Berkovic Kate V Everett Mark R Gardiner Carla Marini Renzo Guerrini Anna-Elina Lehesjoki Auli Siren Michel Guipponi Alain Malafosse Pierre Thomas Rima Nabbout Stephanie Baulac Eric Leguern Rosa Guerrero Jose M Serratosa Philipp S Reif Felix Rosenow Martina Mörzinger Martha Feucht Fritz Zimprich Claudia Kapser Christoph J Schankin Arvid Suls Katrin Smets Peter De Jonghe Albena Jordanova Hande Caglayan Zuhal Yapici Destina A Yalcin Betul Baykan Nerses Bebek Ugur Ozbek Christian Gieger Heinz-Erich Wichmann Tobias Balschun David Ellinghaus Andre Franke Christian Meesters Tim Becker Thomas F Wienker Anne Hempelmann Herbert Schulz Franz Rüschendorf Markus Leber Steffen M Pauck Holger Trucks Mohammad R Toliat Peter Nürnberg Giuliano Avanzini Bobby P C Koeleman Thomas Sander

Genetic generalized epilepsies (GGEs) have a lifetime prevalence of 0.3% and account for 20-30% of all epilepsies. Despite their high heritability of 80%, the genetic factors predisposing to GGEs remain elusive. To identify susceptibility variants shared across common GGE syndromes, we carried out a two-stage genome-wide association study (GWAS) including 3020 patients with GGEs and 3954 contro...

2012
Z Sterjev G Kiteva E Cvetkovska I Petrov I Kuzmanovski TJ Ribarska KA Nestorovska N Matevska S Trajkovik-Jolevska AJ Dimovski Lj Suturkova

Carbamazepine (CBZ) blocks neuronal sodium channels in a voltage- and frequency-dependent manner, delaying the recovery of the channels from the inactivated state, reducing the number of action potentials within a burst, and decreasing burst duration. The α-subunit of the first neuronal sodium channel (SCN1A) is a major gene in different epilepsies. A synonymous polymorphism (SCN1A IVS5N + 5 G>...

Journal: :The Journal of pharmacology and experimental therapeutics 2013
John C Oakley Alvin R Cho Christine S Cheah Todd Scheuer William A Catterall

Seizures remain uncontrolled in 30% of patients with epilepsy, even with concurrent use of multiple drugs, and uncontrolled seizures result in increased morbidity and mortality. An extreme example is Dravet syndrome (DS), an infantile-onset severe epilepsy caused by heterozygous loss of function mutations in SCN1A, the gene encoding the brain type-I voltage-gated sodium channel NaV1.1. Studies ...

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2009
Gustavo A Patino Lieve R F Claes Luis F Lopez-Santiago Emily A Slat Raja S R Dondeti Chunling Chen Heather A O'Malley Charles B B Gray Haruko Miyazaki Nobuyuki Nukina Fumitaka Oyama Peter De Jonghe Lori L Isom

Dravet syndrome (also called severe myoclonic epilepsy of infancy) is one of the most severe forms of childhood epilepsy. Most patients have heterozygous mutations in SCN1A, encoding voltage-gated sodium channel Na(v)1.1 alpha subunits. Sodium channels are modulated by beta1 subunits, encoded by SCN1B, a gene also linked to epilepsy. Here we report the first patient with Dravet syndrome associa...

Journal: :The Canadian journal of neurological sciences. Le journal canadien des sciences neurologiques 2016
Mary B Connolly

Dravet syndrome is one of the most severe epilepsy syndromes of early childhood, and it comes with very high morbidity and mortality. The typical presentation is characterized by hemiclonic or generalized clonic seizures triggered by fever during the first year of life, followed by myoclonic, absence, focal and generalized tonic-clonic seizures. Non-convulsive status epilepticus and epileptic e...

Journal: :Epilepsy currents 2011
Elinor Ben-Menachem

Commentary Imagine you have an adorable baby, the birth went well, and he/she is developing nicely; laughing, smiling, making eye contact, and playing. You are worried because you heard about complications from immunizations, but your pediatri-cian reassures you. In fact, all of your friends have immunized their children without problem. After the injection, your baby has a fever and experience...

Journal: :Seminars in neurology 2015
Ingo Helbig

Generalized epilepsies, particularly the idiopathic or genetic generalized epilepsies (GGEs), represent some of the most common epilepsies. Clinical genetic data including family studies and twin studies provide compelling evidence for a prominent genetic impact. The first decade of the 21st century was marked by progress in understanding the basic biology of generalized epilepsies including ge...

Journal: :Journal of the neurological sciences 2014
Marta Vila-Pueyo Roser Pons Miquel Raspall-Chaure Anna Marcé-Grau Oriel Carreño Cèlia Sintas Bru Cormand Mercè Pineda-Marfà Alfons Macaya

Alternating hemiplegia of childhood (AHC) is a rare neurodevelopmental disorder featuring attacks of hemiplegia and other paroxysmal and non-paroxysmal manifestations leading to progressive neurological impairment. De novo mutations in ATP1A3 have been identified in up to 80% of patients. AHC is also associated with rare mutations in other genes involved in episodic neurological disorders. We s...

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