نتایج جستجو برای: fabry disease

تعداد نتایج: 1493456  

Journal: :European journal of medicinal chemistry 2016
Wei-Chieh Cheng Jen-Hon Wang Huang-Yi Li Sheng-Jhih Lu Jia-Ming Hu Wen-Yi Yun Cheng-Hsin Chiu Wen-Bin Yang Yin-Hsiu Chien Wuh-Liang Hwu

A unique molecular library consisting of all sixteen synthetic ADMDP (1-aminodeoxy-DMDP) stereoisomers has been prepared and evaluated for inhibitory activity against α-Gal A, and ability to impart thermal stabilization of this enzyme. The results of this testing led us to develop a novel pharmacological chaperone for the treatment of Fabry disease. 3-Epimer ADMDP was found to be an effective p...

Journal: :Arquivos brasileiros de oftalmologia 2011
Fabio Yamasato Yonamine Tiago Eugênio Faria e Arantes Cristina Muccioli

Fabry disease is an X-linked disease of glycosphingolipid (GL) metabolism. The accumulation of GL in tissues can affect multiple organ systems. Initial symptoms includes episodes of severe pain in the extremities, cornea verticillata and skin lesions. In late stages, kidney, heart and brain can be involved. This report attempts for importance of cornea verticillata in the diagnosis of Fabry dis...

2015
H Trimarchi R Canzonieri A Muryan A Schiel A Araoz M Forrester A Karl F Lombi J Andrews V Pomeranz T Rengel E Zotta

The time for starting a patient with Fabry disease on enzyme replacement therapy is still a matter of debate, particularly when no overt classical clinical signs or symptoms are present. With respect to Fabry nephropathy, a dual problem coexists: the reluctance of many nephrologists to start enzyme replacement infusion until signs of renal disease appear as the appearance of proteinuria or an e...

Journal: :Circulation. Cardiovascular genetics 2014
Markus Niemann Arndt Rolfs Stefan Störk Bart Bijnens Frank Breunig Meinrad Beer Georg Ertl Christoph Wanner Frank Weidemann

BACKGROUND Currently, no method is available to identify α-galactosidase A (agalA) mutations determining clinically relevant Fabry disease. In our largest European Fabry cohort, we investigated whether a biomarker, specific for the defect, could stratify persons at risk. METHODS AND RESULTS A total of 124 individuals with agalA mutations were investigated with a comprehensive clinical workup,...

Journal: :Journal of Neuropathology & Experimental Neurology 2019

2011
Uma Ramaswami

Fabry disease (FD) is an X-linked lysosomal storage disorder that affects both men and women. The manifestations of this heterogeneous disease are multisystemic and progressive. Prior to the development of enzyme replacement therapy, the management and treatment for Fabry disease was largely nonspecific and supportive. Because enzyme replacement therapy became commercially available in 2001, a ...

2014
Shawn E Lipinski Ozlem Goker-Alpan

2014 Enzyme replacement therapies substitute particular enzymes in individuals who have deficient or absent levels of enzymatic activity due to inherited defects. Fabry disease, a rare X-linked genetic disorder yet common lysosomal storage disease, is due to the impaired activity of alpha-galactosidase A. Currently, there are two enzyme preparations available for the treatment of Fabry disease:...

Journal: :Neuroimmunology and Neuroinflammation 2016

Journal: :International Journal of Molecular Sciences 2020

Journal: :Neuromuscular Diseases 2015

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