نتایج جستجو برای: dysmorphism

تعداد نتایج: 823  

Journal: :Nanoscale 2015
Aibing Chen Yifeng Yu Rujie Wang Yunhong Yu Wenwei Zang Pei Tang Ding Ma

A nanocasting method to fabricate nitrogen-doped dual mesoporous carbon is proposed by the carbonization of nitrile functional ionic liquid (FIL) grafted SBA-15 for the first time. These carbon materials have high nitrogen content (12.8%), large specific surface areas (763 m(2) g(-1)) and uniform rod morphologies, which are derived from FILs grafted on the surface of SBA-15. Furthermore, by adj...

2010
Indrani S. Bhattacharya Marc Dweck Andrew Gardner Mark Jones Mark Francis

Isolated ventricular non-compaction cardiomyopathy (IVNC) is a rare, morphologically distinct primary genetic cardiomyopathy, which is now gaining prominence as an important differential diagnosis in patients presenting with cardiac failure. We describe a case report of a Nigerian male with facial dysmorphism presenting with cardiac failure. This is followed by a review of the literature with f...

Journal: :Journal of medical genetics 1993
G Valkova M Stefanova

Two cases of 14q proximal partial trisomy in sisters from the same family are reported. Clinical features included craniofacial dysmorphism, skin depigmentation, slight anomalies of the limbs, muscular hypertonia, and physical and mental retardation. The third sister had an abnormal phenotype, different from that of her sibs, and proved to be a carrier of a balanced translocation (2;14)(q36;q21...

2016
Jennifer Carter Melinda Zombor Adrienn Máté László Sztriha Jonathan J. Waters

A 10-year-old boy was referred with developmental delay and dysmorphism. Genomewide aCGH microarray analysis detected a de novo 3.7 Mb deletion at 1q32.1: arr 1q32.1(199,985,888-203,690,832)x1 dn [build HG19]. This first report of a deletion in this region implies a critical role for dosage-sensitive genes within 1q32.1 in neurological development. This is consistent with previously reported du...

Journal: :The Canadian journal of neurological sciences. Le journal canadien des sciences neurologiques 2012
Naif Alghasab A Bruce Janati Aslam Khan

middleeast in children of consanguineous parents1. it is a rare autosomal recessive disorder known also as middle-east syndrome or Richadson-Kirk syndrome or hypoparathyroidism -retardation-dysmorphism (HRd) syndrome2. Children afflicted with this condition are born with intrauterine growth retardation, and present with hypocalcemic tetany or seizures due to hypoparathyroidism at an early stage...

2016
Frederike Leonie Harms Katta Mohan Girisha Andrew A. Hardigan Anju Shukla Malik Alawi Ashwin Dalal Lauren Brady Lynne M. Bird Sophia Ceulemans Martina Bebin Susan M. Hiatt Edward J. Lose Michelle Primiano Wendy K. Chung Jane Juusola Zeynep C. Akdemir Matthew Bainbridge Wu-Lin Charng Mohammad K. Eldomery Ayman W. El-Hattab M. Saleh Stéphane Bézieau Benjamin Cogné Bertrand Isidor Sébastien Küry James R. Lupski Richard M. Myers Gregory M. Cooper Kerstin Kutsche

76 From a GeneMatcher-enabled international collaboration, we identified ten individuals with 77 intellectual disability, speech delay, ataxia and facial dysmorphism and a mutation in EBF3, 78 encoding a transcription factor required for neuronal differentiation. Structural assessments, 79 transactivation assays, in situ fractionation, RNA-seq and ChIP-seq experiments collectively 80 show that ...

Journal: :Neuropathology : official journal of the Japanese Society of Neuropathology 2012
Atsushi Sasaki Kei Shioda Taku Homma Ryo Fukatsu Hiroyoshi Koide

The patient was born at 38 weeks gestation with body weight of 2700 g from non-consanguineous parents. She was the third child with two healthy brothers. At 2 months of age, she had afebrile seizures. She was admitted to hospital because of an epileptic state. Her chromosomal pattern was 46XX by G-band analysis. A deletion in the Miller-Dieker syndrome (MDS) region was confirmed by fluorescence...

2014
Isy Lima Peixoto Ana Maria Carreno Vania Mesquita Gadelha Prazeres Caroline Albuquerque Rodrigues Chirano Gabriel Maroja Ihara Patricia Bandeira de Melo Akel

Costello syndrome (CS) is a rare genetic disorder, first described by Costello in 1971, caused by mutations in the HRAS proto-oncogene. Clinical findings include facial dysmorphism, skin disorders, cognitive impairment, cardiac and musculoskeletal defects. There is an increased risk of malignancies in these patients, due to the proto-oncogene mutation, and also sudden death secondary to heart d...

Journal: :Journal of medical genetics 1987
D Kumar P R Heath C E Blank

A patient with a small deletion of the short arm and a partial duplication of the long arm of chromosome 5 is described. The main clinical features include craniofacial dysmorphism, growth failure, developmental retardation, and congenital heart defect. The mother and male sib each carried an inv(5) (p15.3q35) but were phenotypically normal. The possible clinical manifestations of partial dupli...

Journal: :Journal of medical genetics 1988
M L Merrer M L Briard S Girard N Mulliez C Moraine M C Imbert

We report eight cases of a lethal association of failure to thrive, facial dysmorphism, ambiguous genitalia, syndactyly, postaxial polydactyly, and internal developmental anomalies (Hirschsprung's disease, cardiac and renal malformation). This syndrome is likely to be autosomal recessive and resembles Smith-Lemli-Opitz (SLO) syndrome. However, the lethality, the common occurrence of polydactyly...

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