نتایج جستجو برای: smn1

تعداد نتایج: 481  

2017
Eric W. Ottesen Joonbae Seo Natalia N. Singh Ravindra N. Singh

Humans carry two nearly identical copies of Survival Motor Neuron gene: SMN1 and SMN2. Mutations or deletions of SMN1, which codes for SMN, cause spinal muscular atrophy (SMA), a leading genetic disease associated with infant mortality. Aberrant expression or localization of SMN has been also implicated in other pathological conditions, including male infertility, inclusion body myositis, amyot...

2011
Adele D'Amico Eugenio Mercuri Francesco D Tiziano Enrico Bertini

Spinal muscular atrophy (SMA) is an autosomal recessive neuromuscular disease characterized by degeneration of alpha motor neurons in the spinal cord, resulting in progressive proximal muscle weakness and paralysis. Estimated incidence is 1 in 6,000 to 1 in 10,000 live births and carrier frequency of 1/40-1/60. This disease is characterized by generalized muscle weakness and atrophy predominati...

Journal: :The Korean journal of laboratory medicine 2010
Seoyoung Yoon Chang Hoon Lee Kyung-A Lee

Determination of the copy number of the survival motor neuron (SMN) gene is important for detecting spinal muscular atrophy (SMA) carriers and compound heterozygous patients. Multiplex ligationdependent probe amplification (MLPA) assay is a simple and efficient technique used for detecting variations in the copy numbers of different genes. Race- and ethnicity-based variation in the SMA carrier ...

2016
Modibo Sangare Ilo Dicko Cheick Oumar Guinto Adama Sissoko Kekouta Dembele Youlouza Coulibaly Siaka Y. Coulibaly Guida Landoure Abdallah Diallo Mamadou Dolo Housseini Dolo Boubacar Maiga Moussa Traore Mamadou Karembe Kadiatou Traore Amadou Toure Mariam Sylla Arouna Togora Souleymane Coulibaly Sékou Fantamady Traore Brant Hendrickson Katherine Bricceno Alice B. Schindler Angela Kokkinis Katherine G. Meilleur Hammadoun Ali Sangho Brehima Diakite Yaya Kassogue Yaya Ibrahim Coulibaly Barrington Burnett Youssoufa Maiga Seydou Doumbia Kenneth H. Fischbeck

Introduction Spinal muscular atrophy (SMA) and sporadic amyotrophic lateral sclerosis (SALS) are both motor neuron disorders. SMA results from the deletion of the survival motor neuron (SMN) 1 gene. High or low SMN1 copy number and the absence of SMN2 have been reported as risk factors for the development or severity of SALS. Objective To investigate the role of SMN gene copy number in the on...

ژورنال: :genetics in the 3rd millennium 0
زهرا گلکار zahra golkar ماندانا حسن زاد mandana hassan zad واله هادوی valeh hadavi رکسانا کریمی نژاد roxana kariminejad سید نوید المدنی seyed navid almadani فریبا افروزان fariba afroozan بیتا بزرگمهر

آتروفی نخاعی-ماهیچه ای (sma) یکی از بیماری های شایع عصبی-ماهیچه ای، همراه با فلج پیشرونده است که به علت ضایعاتی در نورون حرکتی آلفا در نخاع ایجاد می شود. sma توسط دو ژن smn1 و smn2 بیان می شود که تنها در اگزون شماره 7 خود در یک نوکلئوتید متفاوت هستند. شایع ترین جهش دیده شده حذف هوموزیگوس اگزون 7 در ژن smn1 است. درصد کمی از بیماران هتروزیگوسیتی مرکب با جهش نقطه ای در یک آلل و حذف در آلل دیگر دار...

Journal: :Arquivos De Neuro-psiquiatria 2023

Case presentation: Male patient whose hypotonia was observed around 2 months-old. He diagnosed with Spinal Muscular Atrophy (SMA) when he 4 months-old - heterozygous deletion of the SMN1 gene (1 copy exon 7 and 8), copies SMN2 (2 8 8). In SMN1, a p.Pro246Thrfs*10 variant is observed, characterizing compound heterozygosity. This always had has an excellent multidisciplinary follow-up – motor res...

Journal: :Cell 2012
Francesco Roselli Pico Caroni

How deficiency in SMN1 selectively affects motoneurons in spinal muscular atrophy is poorly understood. Here, Imlach et al. and Lotti et al. show that aberrant splicing of Stasimon in cholinergic sensory neurons and interneurons leads to motoneuron degeneration, suggesting that altered circuit function may underlie the disorder.

Journal: :Annals of the Academy of Medicine, Singapore 2007
Pupak Derakhshandeh-Peykar Mohsen Esmaili Zahra Ousati-Ashtiani Manijeh Rahmani Farbod Babrzadeh Shahla Farshidi Elham Attaran Mohammad Mehdi Sajedifar Dariush Daneshvar Farhud

INTRODUCTION Childhood-onset proximal spinal muscular atrophies (SMAs) are an autosomal recessive, clinically heterogeneous group of neuropathies characterised by the selective degeneration of anterior horn cells. SMA has an estimated incidence of 1 in 10,000 live births. The causative genes are survival motor neuron (SMN) gene and neuronal apoptosis inhibitory protein (NAIP) gene. Deletions of...

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