نتایج جستجو برای: scn1a mutations

تعداد نتایج: 173129  

2016
J. Hsiao T.Y. Yuan M.S. Tsai C.Y. Lu Y.C. Lin M.L. Lee S.W. Lin F.C. Chang H. Liu Pimentel C. Olive C. Coito G. Shen M. Young T. Thorne M. Lawrence M. Magistri M.A. Faghihi O. Khorkova C. Wahlestedt

Dravet syndrome is a devastating genetic brain disorder caused by heterozygous loss-of-function mutation in the voltage-gated sodium channel gene SCN1A. There are currently no treatments, but the upregulation of SCN1A healthy allele represents an appealing therapeutic strategy. In this study we identified a novel, evolutionary conserved mechanism controlling the expression of SCN1A that is medi...

2017
Michael F Hammer Atsushi Ishii Laurel Johnstone Alexander Tchourbanov Branden Lau Ryan Sprissler Brian Hallmark Miao Zhang Jin Zhou Joseph Watkins Shinichi Hirose

Dravet syndrome (DS) is a rare, devastating form of childhood epilepsy that is often associated with mutations in the voltage-gated sodium channel gene, SCN1A. There is considerable variability in expressivity within families, as well as among individuals carrying the same primary mutation, suggesting that clinical outcome is modulated by variants at other genes. To identify modifier gene varia...

Journal: :Epilepsy currents 2014
Gustavo A Patino Jack M Parent

Commentary Dravet syndrome (DS) is a severe pediatric epilepsy that presents with multiple seizure types commonly resistant to pharmacologic treatment, as well as intellectual disability, behavioral abnormalities, gait and motor dysfunction, and increased mortality (1). In most cases, the disease is caused by heterozygous de novo mutations or gene deletions of SCN1A, the gene encoding the pore-...

Journal: :iranian journal of basic medical sciences 0
soha namazi clinical neurology research center, shiraz university of medical sciences, shiraz, iran department of pharmacotherapy, school of pharmacy, shiraz university of medical sciences, shiraz, iran negar azarpira transplant research center, shiraz university of medical sciences, shiraz, iran katayoon javidnia department of medicinal chemistry, school of pharmacy, shiraz university of medical sciences, shiraz, iran mehrdad emami transgenic technology research center, shiraz university of medical sciences, shiraz, iran rahimeh rahjoo department of pharmacotherapy, school of pharmacy, shiraz university of medical sciences, shiraz, iran

objective (s): from a genetic point of view, epilepsy is a polygenic multifactorial syndrome. the scn1a and b genes belong to a family of genes that provide instructions for making sodium channels. understanding the relevance of scn1a and scn1b gene polymorphisms to plasma concentration of carbamazepine (cbz) and its active metabolite carbamazepine 10, 11 epoxide (cbze), may shed more light on ...

2017
Lynette G. Sadleir Emily I. Mountier Deepak Gill Suzanne Davis Charuta Joshi Catherine DeVile Manju A. Kurian Simone Mandelstam Elaine Wirrell Katherine C. Nickels Hema R. Murali Gemma Carvill Candace T. Myers Heather C. Mefford Ingrid E. Scheffer

OBJECTIVE To define a distinct SCN1A developmental and epileptic encephalopathy with early onset, profound impairment, and movement disorder. METHODS A case series of 9 children were identified with a profound developmental and epileptic encephalopathy and SCN1A mutation. RESULTS We identified 9 children 3 to 12 years of age; 7 were male. Seizure onset was at 6 to 12 weeks with hemiclonic s...

Afshin Borhani-Haghighi, Katayoon Javidnia Mehrdad Emami Negar Azarpira, Rahimeh Rahjoo Razieh Berahmand, Soha Namazi,

Objective (s): From a genetic point of view, epilepsy is a polygenic multifactorial syndrome. The SCN1A and B genes belong to a family of genes that provide instructions for making sodium channels. Understanding the relevance of SCN1A and SCN1B gene polymorphisms to plasma concentration of carbamazepine (CBZ) and its active metabolite carbamazepine 10, 11 epoxide (CBZE), may shed more light on ...

Journal: :Pharmacogenomics 2013
Batoul Sadat Haerian Larry Baum Patrick Kwan Hui Jun Tan Azman Ali Raymond Zahurin Mohamed

AIM Approximately a third of newly diagnosed epilepsy patients do not respond to antiepileptic drugs (AEDs). Evidence suggests that low penetrance variants in the genes of drug targets such as voltage-gated sodium channels may be involved in drug responsiveness. To examine this hypothesis, we compared data from two epilepsy cohorts from Malaysia and Hong Kong, as well as a meta-analysis from pu...

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