نتایج جستجو برای: polg gene

تعداد نتایج: 1141492  

2018
Junhua Cao Hongwei Wu Zhenguang Li

Mitochondrial disorders are amongst the most common groups of inborn errors of metabolism. They are caused by deficiencies in the final pathway of the cellular energy production, the mitochondrial respiratory chain. The disorders are clinically and genetically heterogeneous and the aetiology could be found in the mitochondrial, or in the nuclear genome. We searched important e-databases for the...

Journal: :Research results in pharmacology 2021

Introduction: PolG-alpha is a nuclear-encoded enzyme which provides replication and repair of mitochondrial DNA. D257A mutation leads to change in the N-terminal ”proofreading” domain, deprives 3?-5? exonuclease activity, resulting accumulation mutations genome.
 Materials methods: Murine zygotes were microinjected with transgene construction carrying mutant murine Polg coding sequence GFP...

2017
Omar Hikmat Tom Eichele Charalampos Tzoulis Laurence A. Bindoff

Epilepsy is common in polymerase gamma (POLG) related disease and is associated with high morbidity and mortality. Epileptiform discharges typically affect the occipital regions initially and focal seizures, commonly evolving to bilateral convulsive seizures which are the most common seizure types in both adults and children. Our work has shown that mtDNA depletion-i.e., the quantitative loss o...

Journal: :Human molecular genetics 2011
Matthew J Young Matthew J Longley Fang-Yuan Li Rajesh Kasiviswanathan Lee-Jun Wong William C Copeland

Defects in mitochondrial DNA (mtDNA) maintenance comprise an expanding repertoire of polymorphic diseases caused, in part, by mutations in the genes encoding the p140 mtDNA polymerase (POLG), its p55 accessory subunit (POLG2) or the mtDNA helicase (C10orf2). In an exploration of nuclear genes for mtDNA maintenance linked to mitochondrial disease, eight heterozygous mutations (six novel) in POLG...

Journal: :Clinical chemistry 2010
David Dimmock Lin-Ya Tang Eric S Schmitt Lee-Jun C Wong

BACKGROUND The mitochondrial DNA (mtDNA) depletion syndromes (MDDSs) are autosomal recessive disorders characterized by a reduction in cellular mtDNA content. Mutations in at least 9 genes [POLG, polymerase (DNA directed), gamma; DGUOK, deoxyguanosine kinase; TK2, thymidine kinase, mitochondrial; TYMP, thymidine phosphorylase; MPV17, MpV17 mitochondrial inner membrane protein; SUCLA2, succinate...

2017
Enrico Bugiardini Olivia V. Poole Andreea Manole Alan M. Pittman Alejandro Horga Iain Hargreaves Cathy E. Woodward Mary G. Sweeney Janice L. Holton Jan-Willem Taanman Gordon T. Plant Joanna Poulton Massimo Zeviani Daniele Ghezzi John Taylor Conrad Smith Carl Fratter Meena A. Kanikannan Arumugam Paramasivam Kumarasamy Thangaraj Antonella Spinazzola Ian J. Holt Henry Houlden Michael G. Hanna Robert D.S. Pitceathly

OBJECTIVE Pathologic ribonuclease H1 (RNase H1) causes aberrant mitochondrial DNA (mtDNA) segregation and is associated with multiple mtDNA deletions. We aimed to determine the prevalence of RNase H1 gene (RNASEH1) mutations among patients with mitochondrial disease and establish clinically meaningful genotype-phenotype correlations. METHODS RNASEH1 was analyzed in patients with (1) multiple ...

2012

To newly identify loci for age at natural menopause, we carried out a meta-analysis of 22 genome-wide association studies (GWAS) in 38,968 women of European descent, with replication in up to 4,435 women. In addition to four known loci, we identified 3 loci newly associated with age at natural menopause (at P < 5 × 0−8). Candidate genes located at these newly associated loci include genes impli...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید