نتایج جستجو برای: globoid cell leukodystrophy

تعداد نتایج: 1684780  

2017
Yuki Miyamoto Tomohiro Torii Kazuko Kawahara Nanami Hasegawa Akito Tanoue Yoichi Seki Takako Morimoto Megumi Funakoshi-Tago Hiroomi Tamura Keiichi Homma Masahiro Yamamoto Junji Yamauchi

Hypomyelinating leukodystrophy (HLD) is genetic demyelinating or dysmyelinating disease and is associated with at least 13 responsible genes. The mutations seem likely cause the functional deficiency of their gene products. HLD4- and HLD5-associated HSPD1 and FAM126A mutations affect biochemical properties of the gene products (Miyamoto et al. (2015,2014) [[1], [2]]). Herein we provide the data...

2017
Neda Golchin Mohammadreza Hajjari Reza Azizi Malamiri Majid Aminzadeh Javad Mohammadi-asl

Metachromatic leukodystrophy disorder (MLD) is an autosomal recessive and lysosomal storage disease. The disease is caused by the deficiency of the enzyme arylsulfatase A (ARSA) which is encoded by the ARSA gene. Different mutations have been reported in different populations. The present study was aimed to detect the mutation type of the ARSA gene in three relative Iranian patients. We found a...

Journal: :Current opinion in neurology 2010
Wolfgang Köhler

PURPOSE OF REVIEW Knowledge of the metabolic and genetic basis of known and previously unknown leukodystrophies is constantly increasing, opening new treatment options such as enzyme replacement or cell-based therapies. This brief review highlights some recent work, particularly emphasizing results from studies in adulthood leukodystrophies. RECENT FINDINGS Evidence from recent studies sugges...

Journal: :Archives of Disease in Childhood 1973

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2015
Jacqueline A Hawkins-Salsbury Lauren Shea Xuntian Jiang Daniel A Hunter A Miguel Guzman Adarsh S Reddy Elizabeth Y Qin Yedda Li Steven J Gray Daniel S Ory Mark S Sands

Globoid cell leukodystrophy (GLD, Krabbe disease) is a lysosomal storage disease (LSD) caused by a deficiency in galactocerebrosidase (GALC) activity. In the absence of GALC activity, the cytotoxic lipid, galactosylsphingosine (psychosine), accumulates in the CNS and peripheral nervous system. Oligodendrocytes and Schwann cells are particularly sensitive to psychosine, thus leading to a demyeli...

2013
Adarsh S. Reddy Jigisha R. Patel Carole Vogler Robyn S. Klein Mark S. Sands

Globoid-cell Leukodystrophy (GLD; Krabbe's disease) is a rapidly progressing inherited demyelinating disease caused by a deficiency of the lysosomal enzyme Galactosylceramidase (GALC). Deficiency of GALC leads to altered catabolism of galactosylceramide and the cytotoxic lipid, galactosylsphingosine (psychosine). This leads to a rapidly progressive fatal disease with spasticity, cognitive disab...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2010
Xing-Li Meng Jin-Song Shen Shiho Kawagoe Toya Ohashi Roscoe O Brady Yoshikatsu Eto

Most lysosomal storage diseases (LSDs) are life-threatening genetic diseases. The pathogenesis of these diseases is poorly understood. Induced pluripotent stem (iPS) cell technology offers new opportunities for both mechanistic studies and development of stem cell- based therapies. Here we report the generation of disease-specific iPS cells from mouse models of Fabry disease, globoid cell leuko...

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