نتایج جستجو برای: als gene

تعداد نتایج: 1166211  

Journal: :Neurology 2012
Orla Hardiman Denise A Figlewicz

Neurology 2012;79:842–843 Amyotrophic lateral sclerosis (ALS) is a progressive neurodegenerative condition of upper and lower motor neurons. Clinical presentation is heterogeneous and is usually segregated by site of onset (bulbar vs spinal). Extreme phenotypes with better prognosis include primary lateral sclerosis (PLS) (pure upper motor neuron involvement) and progressive muscular atrophy (P...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2010
Bryan J Traynor Michael Nalls Shiao-Lin Lai Raphael J Gibbs Jennifer C Schymick Sampath Arepalli Dena Hernandez Marcel P van der Brug Janel O Johnson Allissa Dillman Mark Cookson Cristina Moglia Andrea Calvo Gabriella Restagno Gabriele Mora Adriano Chiò

It was recently reported that rs1541160 on chromosome 1q24.2 has a marked effect on survival of amyotrophic lateral sclerosis (ALS) patients by influencing KIFAP3 expression. The cohorts used in that study were collected from ALS specialty clinics. We attempted to replicate these findings in a population-based cohort of 504 Italian ALS patients. None of 140 SNPs genotyped within the KIFAP3 locu...

2013
Allison S Limpert Margrith E Mattmann Nicholas D P Cosford

Amyotrophic lateral sclerosis (ALS) is a fatal neurodegenerative disorder with few therapeutic options. While several gene mutations have been implicated in ALS, the exact cause of neuronal dysfunction is unknown and motor neurons of affected individuals display numerous cellular abnormalities. Ongoing efforts to develop novel ALS treatments involve the identification of small molecules targeti...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 1999
P R Beetham P B Kipp X L Sawycky C J Arntzen G D May

Self-complementary chimeric oligonucleotides (COs) composed of DNA and modified RNA residues were evaluated as a means to (i) create stable, site-specific base substitutions in a nuclear gene and (ii) introduce a frameshift in a nuclear transgene in plant cells. To demonstrate the creation of allele-specific mutations in a member of a gene family, COs were designed to target the codon for Pro-1...

HJ Kim JJ Sung KW Lee M Kim WM Cho YH Hong

Amyotrophic lateral sclerosis (ALS) is a neurodegenerative disorder characterized by the progressive loss of motor neurons leading to paralysis and death. Mutations of the human Cu/Zn superoxide dismutase (SOD1) are found in some cases of familial ALS (fALS). Recent evidences suggest the accumulation of intracellular calcium is one of the primary mechanisms of motor neuronal degeneration. In th...

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2002
Li-Jun Wang Yan-Yan Lu Shin-ichi Muramatsu Kunihiko Ikeguchi Ken-ichi Fujimoto Takashi Okada Hiroaki Mizukami Takashi Matsushita Yutaka Hanazono Akihiro Kume Toshiharu Nagatsu Keiya Ozawa Imaharu Nakano

Amyotrophic lateral sclerosis (ALS) is a relentlessly progressive lethal disease that involves selective annihilation of motoneurons. Glial cell line-derived neurotrophic factor (GDNF) is proposed to be a promising therapeutic agent for ALS and other motor neuron diseases. Because adeno-associated virus (AAV) has been developed as an attractive gene delivery system with proven safety, we explor...

Journal: :Folia neuropathologica 2004
Paweł Grieb

Amyotrophic lateral sclerosis (ALS), the most frequent paralytic disease of adults, is untreatable and invariably fatal. Up to 20% of ALS cases are inherited (familial, fALS) and associated with mutations, usually of the superoxide dismutase type 1 (SOD-1) gene. This paper shortly reviews the background for and the use of rodent transgenic models of ALS. Silencing the SOD-1 gene does not produc...

2015
Anna Gajowiak Agnieszka Styś Rafał R. Starzyński Aleksandra Bednarz Małgorzata Lenartowicz Robert Staroń Paweł Lipiński

Amyotrophic lateral sclerosis (ALS) is a progressive neurodegenerative disease characterized by degeneration and loss of motor neurons in the spinal cord, brainstem and motor cortex. Up to 10% of ALS cases are inherited (familial, fALS) and associated with mutations, frequently in the superoxide dismutase 1 (SOD1) gene. Rodent transgenic models of ALS are often used to elucidate a complex patho...

Journal: :Reviews in the neurosciences 2010
Sami J Barmada Steven Finkbeiner

Amyotrophic lateral sclerosis (ALS) and frontotemporal dementia (FTD) are late-onset neurodegenerative disorders that are associated with mutations in the TARDBP gene. The product of this gene, TDP-43, has also been identified as the main component of the intracellular inclusions typical of most cases of ALS and FTD. Recent evidence suggests that TDP-43 is essential for proper development and i...

Journal: :Neuron 2010
Janel O. Johnson Jessica Mandrioli Michael Benatar Yevgeniya Abramzon Vivianna M. Van Deerlin John Q. Trojanowski J. Raphael Gibbs Maura Brunetti Susan Gronka Joanne Wuu Jinhui Ding Leo McCluskey Maria Martinez-Lage Dana Falcone Dena G. Hernandez Sampath Arepalli Sean Chong Jennifer C. Schymick Jeffrey Rothstein Francesco Landi Yong-Dong Wang Andrea Calvo Gabriele Mora Mario Sabatelli Maria Rosaria Monsurrò Stefania Battistini Fabrizio Salvi Rossella Spataro Patrizia Sola Giuseppe Borghero Giuliana Galassi Sonja W. Scholz J. Paul Taylor Gabriella Restagno Adriano Chiò Bryan J. Traynor

Using exome sequencing, we identified a p.R191Q amino acid change in the valosin-containing protein (VCP) gene in an Italian family with autosomal dominantly inherited amyotrophic lateral sclerosis (ALS). Mutations in VCP have previously been identified in families with Inclusion Body Myopathy, Paget disease, and Frontotemporal Dementia (IBMPFD). Screening of VCP in a cohort of 210 familial ALS...

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