نتایج جستجو برای: ژن smn1

تعداد نتایج: 16245  

2017
Sumonta Chaisomchit Wanna Thongnoppakhun Theeraphong Pho-iam Chanin Limwongse Surachai Likasitwattanakul Wiyada Chareonsiriwatana Pa-Thai Yenchitsomanus

Spinal muscular atrophy (SMA) is an autosomal recessive genetic disorder, characterized by the degeneration of motor neurons of the spinal cord, thus leading to the deaths of newborns. More than 95% of SMA patients are caused by the absence of survival motor neuron 1 (SMN1) gene exon 7, located on chromosome 5q13. The SMA disease prevalence and SMA mutations in Thailand have never been reported...

Journal: :Current Biology 1999
A. Gregory Matera

Spinal muscular atrophy is caused by mutations in the SMN1 gene, the product of which is part of a multi-component complex involved in the assembly of small nuclear ribonucleoproteins. A recent study indicates that SMN may also play a role in pre-mRNA splicing.

Journal: :Arquivos De Neuro-psiquiatria 2023

Background: Spinal muscular atrophy (SMA) is a genetic motor neuron disease caused by mutations in the SMN1 (Survival Motor Neuron) gene, which leads to hypotonia and muscle weakness with high mortality related respiratory involvement. Gene therapy (GT) (onasemnogeno aberpavovec) for SMA, through an adeno-associated viral vector 9 (AAV9) was recently approved our country, but its safety efficac...

2017
Eric W. Ottesen Joonbae Seo Natalia N. Singh Ravindra N. Singh

Humans carry two nearly identical copies of Survival Motor Neuron gene: SMN1 and SMN2. Mutations or deletions of SMN1, which codes for SMN, cause spinal muscular atrophy (SMA), a leading genetic disease associated with infant mortality. Aberrant expression or localization of SMN has been also implicated in other pathological conditions, including male infertility, inclusion body myositis, amyot...

2011
Adele D'Amico Eugenio Mercuri Francesco D Tiziano Enrico Bertini

Spinal muscular atrophy (SMA) is an autosomal recessive neuromuscular disease characterized by degeneration of alpha motor neurons in the spinal cord, resulting in progressive proximal muscle weakness and paralysis. Estimated incidence is 1 in 6,000 to 1 in 10,000 live births and carrier frequency of 1/40-1/60. This disease is characterized by generalized muscle weakness and atrophy predominati...

Journal: :The Korean journal of laboratory medicine 2010
Seoyoung Yoon Chang Hoon Lee Kyung-A Lee

Determination of the copy number of the survival motor neuron (SMN) gene is important for detecting spinal muscular atrophy (SMA) carriers and compound heterozygous patients. Multiplex ligationdependent probe amplification (MLPA) assay is a simple and efficient technique used for detecting variations in the copy numbers of different genes. Race- and ethnicity-based variation in the SMA carrier ...

2016
Modibo Sangare Ilo Dicko Cheick Oumar Guinto Adama Sissoko Kekouta Dembele Youlouza Coulibaly Siaka Y. Coulibaly Guida Landoure Abdallah Diallo Mamadou Dolo Housseini Dolo Boubacar Maiga Moussa Traore Mamadou Karembe Kadiatou Traore Amadou Toure Mariam Sylla Arouna Togora Souleymane Coulibaly Sékou Fantamady Traore Brant Hendrickson Katherine Bricceno Alice B. Schindler Angela Kokkinis Katherine G. Meilleur Hammadoun Ali Sangho Brehima Diakite Yaya Kassogue Yaya Ibrahim Coulibaly Barrington Burnett Youssoufa Maiga Seydou Doumbia Kenneth H. Fischbeck

Introduction Spinal muscular atrophy (SMA) and sporadic amyotrophic lateral sclerosis (SALS) are both motor neuron disorders. SMA results from the deletion of the survival motor neuron (SMN) 1 gene. High or low SMN1 copy number and the absence of SMN2 have been reported as risk factors for the development or severity of SALS. Objective To investigate the role of SMN gene copy number in the on...

Journal: :Arquivos De Neuro-psiquiatria 2023

Case presentation: Male patient whose hypotonia was observed around 2 months-old. He diagnosed with Spinal Muscular Atrophy (SMA) when he 4 months-old - heterozygous deletion of the SMN1 gene (1 copy exon 7 and 8), copies SMN2 (2 8 8). In SMN1, a p.Pro246Thrfs*10 variant is observed, characterizing compound heterozygosity. This always had has an excellent multidisciplinary follow-up – motor res...

Journal: :Cell 2012
Francesco Roselli Pico Caroni

How deficiency in SMN1 selectively affects motoneurons in spinal muscular atrophy is poorly understood. Here, Imlach et al. and Lotti et al. show that aberrant splicing of Stasimon in cholinergic sensory neurons and interneurons leads to motoneuron degeneration, suggesting that altered circuit function may underlie the disorder.

Journal: :Annals of the Academy of Medicine, Singapore 2007
Pupak Derakhshandeh-Peykar Mohsen Esmaili Zahra Ousati-Ashtiani Manijeh Rahmani Farbod Babrzadeh Shahla Farshidi Elham Attaran Mohammad Mehdi Sajedifar Dariush Daneshvar Farhud

INTRODUCTION Childhood-onset proximal spinal muscular atrophies (SMAs) are an autosomal recessive, clinically heterogeneous group of neuropathies characterised by the selective degeneration of anterior horn cells. SMA has an estimated incidence of 1 in 10,000 live births. The causative genes are survival motor neuron (SMN) gene and neuronal apoptosis inhibitory protein (NAIP) gene. Deletions of...

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