نتایج جستجو برای: ژن fxn

تعداد نتایج: 16212  

2011
Aurélien Bayot Renata Santos Jean-Michel Camadro Pierre Rustin

Friedreich's ataxia, the most frequent progressive autosomal recessive disorder involving the central and peripheral nervous systems, is mostly associated with unstable expansion of GAA trinucleotide repeats in the first intron of the FXN gene, which encodes the mitochondrial frataxin protein. Since FXN was shown to be involved in Friedreich's ataxia in the late 1990s, the consequence of fratax...

2014
Mohammad Hossein Salehi Behnam Kamalidehghan Massoud Houshmand Goh Yong Meng Majid Sadeghizadeh Omid Aryani Shahriar Nafissi

Friedreich ataxia (FRDA) is the most frequent progressive autosomal recessive disorder associated with unstable expansion of GAA trinucleotide repeats in the first intron of the FXN gene, which encodes for the mitochondrial frataxin protein. The number of repeats correlates with disease severity, where impaired transcription of the FXN gene results in reduced expression of the frataxin protein....

Journal: :Iranian biomedical journal 2014
Mohammad Hossein Salehi Massoud Houshmand Omid Aryani Behnam Kamalidehghan Elham Khalili

BACKGROUND Friedreich ataxia (FRDA) is an autosomal recessive disorder caused by guanine-adenine-adenine (GAA) triplet expansions in the FXN gene. Its product, frataxin, which severely reduces in FRDA patients, leads to oxidative damage in mitochondria. The purpose of this study was to evaluate the triple nucleotide repeated expansions in Iranian FRDA patients and to elucidate distinguishable F...

Journal: :Archives of neurology 2012
Mathieu Anheim Louise-Laure Mariani Patrick Calvas Emmanuel Cheuret Fabien Zagnoli Sylvie Odent Claire Seguela Cecilia Marelli Marlène Fritsch Jean-Pierre Delaunoy Alexis Brice Alexandra Dürr Michel Koenig

BACKGROUND Friedreich ataxia (FA) is the most frequent type of autosomal recessive cerebellar ataxia, occurring at a mean age of 16 years. Nearly 98% of patients with FA present with homozygous GAA expansions in the FXN gene. The remaining patients are compound heterozygous for an expansion and a point mutation. Patients who are compound heterozygous for an exonic deletion and an expansion are ...

2015
Michael Lazaropoulos Yina Dong Elisia Clark Nathaniel R Greeley Lauren A Seyer Karlla W Brigatti Carlton Christie Susan L Perlman George R Wilmot Christoper M Gomez Katherine D Mathews Grace Yoon Theresa Zesiewicz Chad Hoyle Sub H Subramony Alicia F Brocht Jennifer M Farmer Robert B Wilson Eric C Deutsch David R Lynch

OBJECTIVE Friedreich ataxia (FRDA) is an autosomal recessive ataxia resulting from mutations in the frataxin gene (FXN). Such mutations, usually expanded guanine-adenine-adenine (GAA) repeats, give rise to decreased levels of frataxin protein in both affected and unaffected tissues. The goal was to understand the relationship of frataxin levels in peripheral tissues to disease status. METHODS...

2017
Ashley McCormick Jennifer Farmer Susan Perlman Martin Delatycki George Wilmot Katherine Matthews Grace Yoon Chad Hoyle Sub H Subramony Theresa Zesiewicz David R Lynch Shana E McCormack

OBJECTIVE Friedreich ataxia (FA) is a progressive neuromuscular disorder caused by GAA triplet repeat expansions or point mutations in the FXN gene. FA is associated with increased risk of diabetes mellitus (DM). This study assessed the age-specific prevalence of FA-associated DM and its impact on neurologic outcomes. RESEARCH DESIGN AND METHODS Participants were 811 individuals with FA from ...

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