نتایج جستجو برای: smn2 protein

تعداد نتایج: 1234838  

2013
Y. Sifi K. Sifi A. Boulefkhad N. Abadi Z. Bouderda R. Cheriet M. Magen J. P. Bonnefont A. Munnich C. Benlatreche A. Hamri

Spinal muscular atrophy (SMA) is the second most common lethal autosomal recessive disorder. It is divided into the acute Werdnig-Hoffmann disease (type I), the intermediate form (type II), the Kugelberg-Welander disease (type III), and the adult form (type IV). The gene involved in all four forms of SMA, the so-called survival motor neuron (SMN) gene, is duplicated, with a telomeric (tel SMN o...

2014
Sunghee Cho Heegyum Moon Tiing Jen Loh Hyun Kyung Oh Hey-Ran Kim Myung-Geun Shin D Joshua Liao Jianhua Zhou Xuexiu Zheng Haihong Shen

Spinal muscular atrophy (SMA) is a human genetic disease which occurs because of the deletion or mutation of SMN1 gene. SMN1 gene encodes the SMN protein which plays a key role in spliceosome assembly. Although human patients contain SMN2, a duplicate of SMN1, splicing of SMN2 produces predominantly exon 7 skipped isoform. In order to understand the functions of splice site sequences on exon 7 ...

Journal: :Human molecular genetics 2009
Faraz Farooq Sylvia Balabanian Xuejun Liu Martin Holcik Alex MacKenzie

Spinal muscle atrophy (SMA) is an autosomal recessive neurodegenerative disease which is characterized by the loss of alpha motor neurons resulting in progressive muscle atrophy. Reduced amount of functional survival motor neuron (SMN) protein due to mutations or deletion in the SMN1 gene is the cause of SMA. A potential treatment strategy for SMA is to upregulate levels of SMN protein originat...

Journal: :Functional neurology 2010
Edmar Zanoteli Jessica Ruivo Maximino Umbertina Conti Reed Gerson Chadi

Spinal muscular atrophy (SMA) is an autosomal recessive disease characterized by degeneration and loss of lower motor neurons in the spinal cord and brainstem. Clinically, SMA has been classified into four types, according to the maximum function attained. The disease is caused by deletion or mutation of the telomeric copy of the SMN gene (SMN1), and the clinical severity is in part determined ...

Journal: :PLoS ONE 2008
Tristan H. Coady Travis D. Baughan Monir Shababi Marco A. Passini Christian L. Lorson

RNA modalities are developing as a powerful means to re-direct pathogenic pre-mRNA splicing events. Improving the efficiency of these molecules in vivo is critical as they move towards clinical applications. Spinal muscular atrophy (SMA) is caused by loss of SMN1. A nearly identical copy gene called SMN2 produces low levels of functional protein due to alternative splicing. We previously report...

2016
Modibo Sangare Ilo Dicko Cheick Oumar Guinto Adama Sissoko Kekouta Dembele Youlouza Coulibaly Siaka Y. Coulibaly Guida Landoure Abdallah Diallo Mamadou Dolo Housseini Dolo Boubacar Maiga Moussa Traore Mamadou Karembe Kadiatou Traore Amadou Toure Mariam Sylla Arouna Togora Souleymane Coulibaly Sékou Fantamady Traore Brant Hendrickson Katherine Bricceno Alice B. Schindler Angela Kokkinis Katherine G. Meilleur Hammadoun Ali Sangho Brehima Diakite Yaya Kassogue Yaya Ibrahim Coulibaly Barrington Burnett Youssoufa Maiga Seydou Doumbia Kenneth H. Fischbeck

Introduction Spinal muscular atrophy (SMA) and sporadic amyotrophic lateral sclerosis (SALS) are both motor neuron disorders. SMA results from the deletion of the survival motor neuron (SMN) 1 gene. High or low SMN1 copy number and the absence of SMN2 have been reported as risk factors for the development or severity of SALS. Objective To investigate the role of SMN gene copy number in the on...

Journal: :RNA 2009
Mafalda Martins de Araújo Sophie Bonnal Michelle L Hastings Adrian R Krainer Juan Valcárcel

Spinal Muscular atrophy is a prevalent genetic disease caused by mutation of the SMN1 gene, which encodes the SMN protein involved in assembly of small nuclear ribonucleoprotein (snRNP) complexes. A paralog of the gene, SMN2, cannot provide adequate levels of functional SMN because exon 7 is skipped in a significant fraction of the mature transcripts. A C to T transition located at position 6 o...

2013
Natalia N. Singh Mariah N. Lawler Eric W. Ottesen Daya Upreti Jennifer R. Kaczynski Ravindra N. Singh

Here, we report a long-distance interaction (LDI) as a critical regulator of alternative splicing of Survival Motor Neuron 2 (SMN2) exon 7, skipping of which is linked to spinal muscular atrophy (SMA), a leading genetic disease of children and infants. We show that this LDI is linked to a unique intra-intronic structure that we term internal stem through LDI-1 (ISTL1). We used site-specific mut...

Journal: :Translational neuroscience 2013
Senthilkumar Sivanesan Matthew D Howell Christine J Didonato Ravindra N Singh

Spinal muscular atrophy (SMA) is the leading genetic cause of infant mortality. SMA results from deletions or mutations of survival motor neuron 1 (SMN1), an essential gene. SMN2, a nearly identical copy, can compensate for SMN1 loss if SMN2 exon 7 skipping is prevented. Among the many cis-elements involved in the splicing regulation of SMN exon 7, intronic splicing silencer N1 (ISS-N1) has eme...

Journal: :Human mutation 2010
Myriam Vezain Pascale Saugier-Veber Elisa Goina Renaud Touraine Véronique Manel Annick Toutain Séverine Fehrenbach Thierry Frébourg Franco Pagani Mario Tosi Alexandra Martins

Spinal muscular atrophy (SMA) is a common neuromuscular disorder caused by homozygous inactivation of the SMN1 (Survival Motor Neuron 1) gene. The disease severity is mainly influenced by the copy number of SMN2, a nearly identical gene from which only low amounts of full-length mRNA are produced. This correlation is not absolute, suggesting the existence of yet unknown factors modulating disea...

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