نتایج جستجو برای: lysosomal disorders

تعداد نتایج: 684439  

Journal: :Clinical chemistry 1998
C T Hua J J Hopwood S R Carlsson R J Harris P J Meikle

For many lysosomal storage disorders, presymptomatic detection, before the onset of irreversible pathology, will greatly improve the efficacy of current and proposed therapies. In the absence of a family history, presymptomatic detection can be achieved only by a comprehensive newborn screening program. Recently we reported that the lysosome-associated membrane protein LAMP-1 was increased in t...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2004
Makoto Yoshimitsu Takeya Sato Kesheng Tao Jagdeep S Walia Vanessa I Rasaiah Gillian T Sleep Gary J Murray Armando G Poeppl John Underwood Lori West Roscoe O Brady Jeffrey A Medin

Successful therapy for many inherited disorders could be improved if the intervention were initiated early. This is especially true for lysosomal storage disorders. Earlier intervention may allow metabolic correction to occur before lipid buildup has irreversible consequences and/or before the immune system mounts limiting responses. We have been developing gene therapy to treat lysosomal stora...

Journal: :Bone 2021

The hips are frequently involved in inheritable diseases which affect the bones. clinical and radiological presentation of these may be very similar to common hip disorders as developmental dysplasia hip, osteoarthritis avascular necrosis, so diagnosis easily overlooked treatment suboptimal. Mucopolysaccharidosis (MPS) Mucolipidosis (ML II III) lysosomal storage with multisystemic involvement. ...

Journal: :Biochimica et Biophysica Acta (BBA) - Molecular Basis of Disease 2008

Journal: :The Journal of biological chemistry 2011
Fan Wang Wensi Song Giovanna Brancati Laura Segatori

Lysosomal storage disorders are often caused by mutations that destabilize native folding and impair trafficking of secretory proteins. We demonstrate that endoplasmic reticulum (ER)-associated degradation (ERAD) prevents native folding of mutated lysosomal enzymes in patient-derived fibroblasts from two clinically distinct lysosomal storage disorders, namely Gaucher and Tay-Sachs disease. Prol...

Journal: :Human molecular genetics 2008
Carmine Settembre Alessandro Fraldi Luca Jahreiss Carmine Spampanato Consuelo Venturi Diego Medina Raquel de Pablo Carlo Tacchetti David C Rubinsztein Andrea Ballabio

Most lysosomal storage disorders (LSDs) are caused by deficiencies of lysosomal hydrolases. While LSDs were among the first inherited diseases for which the underlying biochemical defects were identified, the mechanisms from enzyme deficiency to cell death are poorly understood. Here we show that lysosomal storage impairs autophagic delivery of bulk cytosolic contents to lysosomes. By studying ...

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