نتایج جستجو برای: gaucher type 1

تعداد نتایج: 3648308  

2011
Giacomo Brisca Maja Di Rocco Paolo Picco Maria Beatrice Damasio Alberto Martini

Gaucher disease (GD) type 1 is the most common lysosomal storage disorder due to beta glucocerebrosidase deficiency leading to an abnormal accumulation of its substrate, glucocerebroside, in the mononuclear phagocyte system. The disease presentation is usually characterized by signs and symptoms related to hypersplenism, such as splenomegaly, anaemia, thrombocytopenia and leucopenia. Skeletal d...

Journal: :International Journal of Surgery Case Reports 2016

Journal: :Clinical investigation 2011
Thomas A Burrow Gregory A Grabowski

Gaucher disease is an autosomal recessively inherited lysosomal storage disease that results from the defective activity of the enzyme acid β-glucosidase (glucocerebrosidase). Velaglucerase alfa was recently developed and approved as an alternative form to imiglucerase enzyme therapy. Despite differences in primary structure and glycosylation patterns, recent preclinical and clinical trials of ...

2012
Gaetano Giuffrida Maria Rocca Cingari Nunziatina Parrinello Alessandra Romano Anna Triolo Magda Franceschino Francesco Di Raimondo

Bone complications occur frequently in Gaucher disease (GD) and reduce the quality of life of these patients. Skeletal involvement is an important indication for treatment to ameliorate symptoms and reduce the risk of irreversible and debilitating disease. Bone biomarkers have been used to assess disease status and the response to therapy in a number of bone disorders. Here, we examine the lite...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2014
Pramod K Mistry Jun Liu Li Sun Wei-Lien Chuang Tony Yuen Ruhua Yang Ping Lu Kate Zhang Jianhua Li Joan Keutzer Agnes Stachnik Albert Mennone James L Boyer Dhanpat Jain Roscoe O Brady Maria I New Mone Zaidi

The inherited deficiency of the lysosomal glucocerebrosidase (GBA) due to mutations in the GBA gene results in Gaucher disease (GD). A vast majority of patients present with nonneuronopathic, type 1 GD (GD1). GBA deficiency causes the accumulation of two key sphingolipids, glucosylceramide (GL-1) and glucosylsphingosine (LysoGL-1), classically noted within the lysosomes of mononuclear phagocyte...

Journal: :Journal of medical genetics 1986
J Zlotogora R Zaizov C Klibansky Y Matoth G Bach T Cohen

Considerable clinical variability occurs in adult Gaucher disease type I and three main subtypes may be delineated: a very mild form, a severe form, and a moderate form which itself presents various clinical manifestations. A study based on 25 families from our clinic and a review of published reports showed that when both parents were heterozygous and more than one child was affected with Gauc...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 1998
Y Liu K Suzuki J D Reed A Grinberg H Westphal A Hoffmann T Döring K Sandhoff R L Proia

Gaucher disease is caused by mutations in the gene encoding the lysosomal enzyme glucocerebrosidase (GC). Three clinical types of Gaucher disease have been defined according to the presence (type 2 and 3) or absence (type 1) of central nervous system disease and severity of clinical manifestations. The clinical course of the disease correlates with the mutation carried by the GC gene. To produc...

Journal: :Annals of translational medicine 2015
Simon Wheeler Dan John Sillence

Gaucher disease is caused by mutations in the Gba1 gene encoding an acid β-glucocerebrosidase (GBA1), the lysosomal hydrolase which breaks down glucosylceramide (GlcCer). In Gaucher type 1 disease the accumulation of this simple glycolipid is mainly restricted to tissue phagocyte lysosomes resulting ultimately in hepatomegaly, splenomegaly and osteopenia. Lower residual GBA1 levels leads to neu...

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