نتایج جستجو برای: col6a1

تعداد نتایج: 128  

Journal: :American journal of human genetics 2012
Christine Ackerman Adam E Locke Eleanor Feingold Benjamin Reshey Karina Espana Janita Thusberg Sean Mooney Lora J H Bean Kenneth J Dooley Clifford L Cua Roger H Reeves Stephanie L Sherman Cheryl L Maslen

About half of people with trisomy 21 have a congenital heart defect (CHD), whereas the remainder have a structurally normal heart, demonstrating that trisomy 21 is a significant risk factor but is not causal for abnormal heart development. Atrioventricular septal defects (AVSD) are the most commonly occurring heart defects in Down syndrome (DS), and ∼65% of all AVSD is associated with DS. We us...

2017
Yuelei Jin Huifang Zhu Wei Cai Xiaoyan Fan Yitao Wang Yulong Niu Fangzhou Song Youquan Bu

B-Myb is a transcription factor that is overexpressed and plays an oncogenic role in several types of human cancers. However, its potential implication in lung cancer remains elusive. In the present study, we have for the first time investigated the expression profile of B-Myb and its functional impact in lung cancer. Expression analysis by quantificational real-time polymerase chain reaction (...

2016
Marike M. van Beuge Evert-Jan P. M. ten Dam Paul M. N. Werker Ruud A. Bank

BACKGROUND Dupuytren's disease is a fibroproliferative disease of the hand and fingers, which usually manifests as two different phenotypes within the same patient. The disease first causes a nodule in the palm of the hand, while later, a cord develops, causing contracture of the fingers. RESULTS We set out to characterize the two phenotypes by comparing matched cord and nodule tissue from te...

Journal: :Human molecular genetics 2015
Laetitia Ramanoudjame Claire Rocancourt Jeanne Lainé Arnaud Klein Lucette Joassard Corine Gartioux Marjory Fleury Laura Lyphout Edor Kabashi Sorana Ciura Xavier Cousin Valérie Allamand

Collagen VI (COLVI), a protein ubiquitously expressed in connective tissues, is crucial for structural integrity, cellular adhesion, migration and survival. Six different genes are recognized in mammalians, encoding six COLVI-chains that assemble as two 'short' (α1, α2) and one 'long' chain (theoretically any one of α3-6). In humans, defects in the most widely expressed heterotrimer (α123), due...

2016
Xin Chen Jun Guo Tao Cai Fengshan Zhang Shengfa Pan Li Zhang Shaobo Wang Feifei Zhou Yinze Diao Yanbin Zhao Zhen Chen Xiaoguang Liu Zhongqiang Chen Zhongjun Liu Yu Sun Jie Du

Ossification of the posterior longitudinal ligament of the spine (OPLL), which is characterized by ectopic bone formation in the spinal ligaments, can cause spinal-cord compression. To date, at least 11 susceptibility genes have been genetically linked to OPLL. In order to identify potential deleterious alleles in these OPLL-associated genes, we designed a capture array encompassing all coding ...

2017
Kristin L. Fraser Scott Wong A. Reghan Foley Sameer Chhibber Carsten G. Bönnemann Daniel J. Lesser Carla Grosmann Anne Rutkowski

Collagen VI-related dystrophy (collagen VI-RD) is a rare neuromuscular condition caused by mutations in the COL6A1, COL6A2 or COL6A3 genes. The phenotypic spectrum includes early-onset Ullrich congenital muscular dystrophy, adult-onset Bethlem myopathy and an intermediate phenotype. The disorder is characterised by distal hyperlaxity and progressive muscle weakness, joint contractures and respi...

Journal: :Clinical genetics 2017
H J Park H Jang J H Kim J H Lee H Y Shin S M Kim K D Park S-V Yim J H Lee Y-C Choi

Inherited muscular disorders (IMDs) are clinically and genetically heterogeneous genetic disorders. We investigated the mutational spectrum and genotype-phenotype correlations in Korean patients with IMD. We developed a targeted panel of 69 known IMD genes and recruited a total of 209 Korean patients with IMD. Targeted capture sequencing identified 994 different variants. Among them, 98 variant...

Journal: :genetics in the 3rd millennium 0
zahra , kalhor zohreh fattahi mahsa fadaee raheleh vazehan elham parsimehr

neuromuscular disorders (nmds) include a broad range of diseases affecting muscles, nerves and neuromuscular junctions. approximately 761 different disorders occur in this group which is subdivided into 16 different subgroups with 406 known genes. nmds are genetically and clinically heterogeneous conditions. the advent of next generation sequencing (ngs) approaches has accelerated the pace of d...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید