نتایج جستجو برای: alport syndrome

تعداد نتایج: 622022  

2017
Clifford Kashtan

In this commentary, I review recent advances in Alport syndrome genetics, diagnostics, and therapeutics. I also offer some opinions regarding strategies to optimize the early identification of affected individuals to promote early therapeutic intervention.

Journal: :Nephrology, dialysis, transplantation : official publication of the European Dialysis and Transplant Association - European Renal Association 2010
Michelle N Rheault Stefan M Kren Linda A Hartich Melanie Wall William Thomas Hector A Mesa Philip Avner George E Lees Clifford E Kashtan Yoav Segal

BACKGROUND Female carriers of X-linked Alport syndrome (XLAS) demonstrate variability in clinical phenotype that, unlike males, cannot be correlated with genotype. X-inactivation, the method by which females (XX) silence transcription from one X chromosome in order to achieve gene dosage parity with males (XY), likely modifies the carrier phenotype, but this hypothesis has not been tested direc...

2013
Sumiko I. Armstead Thomas Hellmark Jorgen Wieslander Xin J. Zhou Ramesh Saxena Nilum Rajora

Posttransplant antiglomerular basement membrane (anti-GBM) disease occurs in approximately 5% of Alport patients and usually ends in irreversible graft failure. Recent research has focused on characterizing the structure of the anti-GBM alloepitope. Here we present a case of a 22-year-old male with end-stage renal disease secondary to Alport syndrome, with a previously failed renal allograft, w...

Journal: :Journal of the American Society of Nephrology : JASN 2008
Kan Katayama Mitsuo Kawano Ichiro Naito Hitoshi Ishikawa Yoshikazu Sado Nagisa Asakawa Tomohiro Murata Kazuki Oosugi Michiyo Kiyohara Eiji Ishikawa Masaaki Ito Shinsuke Nomura

Alport syndrome is a hereditary nephropathy that results in irreversible, progressive renal failure. Recent reports suggested that bone marrow transplantation (BMT) has a beneficial, short-term effect on renal injury in Alport (Col4a3(-/-)) mice, but its long-term effects, especially with regard to survival, are unknown. In this study, Alport mice received a transplant of either wild-type or Co...

Journal: :Journal of medical genetics 2002
I Meloni F Vitelli L Pucci R B Lowry R Tonlorenzi E Rossi M Ventura G Rizzoni C E Kashtan B Pober A Renieri

X linked Alport syndrome (ATS, OMIM 301050) is a hereditary glomerulonephritis resulting from either point mutations or intragenic deletions of the COL4A5 gene encoding the α5 chain of type IV collagen. Contiguous gene syndromes are phenotypically complex disorders associated with the deletion of multiple adjacent genes. There are several examples of such syndromes on the X chromosome. 5 Until ...

2017
Oliver Gross Clifford E. Kashtan Michelle N. Rheault Frances Flinter Judith Savige Jeffrey H. Miner Roser Torra Elisabet Ars Constantinos Deltas Isavella Savva Laura Perin Alessandra Renieri Francesca Ariani Francesca Mari Colin Baigent Parminder Judge Bertrand Knebelman Laurence Heidet Sharon Lagas Dave Blatt Jie Ding Yanqin Zhang Daniel P. Gale Marco Prunotto Yong Xue Asher D. Schachter Lori C.G. Morton Jacqui Blem Michael Huang Shiguang Liu Sebastien Vallee Daniel Renault Julia Schifter Jules Skelding Susie Gear Tim Friede A. Neil Turner Rachel Lennon

Alport syndrome (AS) is a genetic disease characterized by haematuric glomerulopathy variably associated with hearing loss and anterior lenticonus. It is caused by mutations in the COL4A3, COL4A4 or COL4A5 genes encoding the α3α4α5(IV) collagen heterotrimer. AS is rare, but it accounts for >1% of patients receiving renal replacement therapy. Angiotensin-converting enzyme inhibition slows, but d...

Journal: :Danish medical bulletin 2009
Jens Michael Hertz

Alport syndrome (AS) is a progressive renal disease that is characterised by hematuria and progressive renal failure, and often accompanied by progressive high-tone sensorineural hearing loss and ocular changes in form of macular flecks and lenticonus. AS is a genetic heterogenous disease, and X-linked dominant in about 85% of the families. The autosomal recessive and dominant forms constitute ...

Journal: :Indian Journal of Ophthalmology 2018

Journal: :Nephrology Dialysis Transplantation 2007

Journal: :Cell Chemical Biology 2018

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