نتایج جستجو برای: بیماری lhon

تعداد نتایج: 44681  

2003
Christophe Orssaud Jean-Louis Dufier

Keywords Disease name and synonyms Excluded diseases Definition/Diagnosis criteria Differential diagnosis Frequency Clinical description Etiology Paraclinic testing and diagnosis Treatment References Abstract Leber's hereditary optic neuropathy (LHON) refers to an optic nerve dysfunction due to mutations in the mitochondrial DNA (mtDNA) and is transmitted in a non-mendelian or maternal pattern....

2009
Matthew Anthony Kirkman Patrick Yu-Wai-Man Alex Korsten Miriam Leonhardt Konstantin Dimitriadis Ireneaus F. De Coo Thomas Klopstock Patrick Francis Chinnery

Leber hereditary optic neuropathy (LHON) is a genetic disorder primarily due to mutations of mitochondrial DNA (mtDNA). Environmental factors are thought to precipitate the visual failure and explain the marked incomplete penetrance of LHON, but previous small studies have failed to confirm this to be the case. LHON has no treatment, so identifying environmental triggers is the key to disease p...

2012
Rui Bi A-Mei Zhang Xiaoyun Jia Qingjiong Zhang Yong-Gang Yao

PURPOSE The majority of Leber hereditary optic neuropathy (LHON) cases are caused by one of three mitochondrial DNA (mtDNA) primary mutations (m.3460G>A, m.11778G>A, and m.14484T>C). In recent studies, we and others have shown that mutation m.3635G>A is a primary LHON mutation, particularly in Chinese. The purpose of this study was to perform a thorough analysis for the complete mtDNA genome se...

2017

Leber's hereditary optic neuropathy (LHON)-plus is a maternally inherited genetic disorder of young males and characterized by severe progressive vision loss with other neurological and systemic symptoms. Here we present a young male with subacute progressive vision loss and Parkinsonism symptoms like right arm rigidity and endocrine abnormalities like hypoparathyroidism as a probable LHON-plus...

2012
Alessandro Achilli Luisa Iommarini Anna Olivieri Maria Pala Baharak Hooshiar Kashani Pascal Reynier Chiara La Morgia Maria Lucia Valentino Rocco Liguori Fabio Pizza Piero Barboni Federico Sadun Anna Maria De Negri Massimo Zeviani Helene Dollfus Antoine Moulignier Ghislaine Ducos Christophe Orssaud Dominique Bonneau Vincent Procaccio Beate Leo-Kottler Sascha Fauser Bernd Wissinger Patrizia Amati-Bonneau Antonio Torroni Valerio Carelli

BACKGROUND Leber's hereditary optic neuropathy (LHON) is a maternally inherited blinding disorder, which in over 90% of cases is due to one of three primary mitochondrial DNA (mtDNA) point mutations (m.11778G>A, m.3460G>A and m.14484T>C, respectively in MT-ND4, MT-ND1 and MT-ND6 genes). However, the spectrum of mtDNA mutations causing the remaining 10% of cases is only partially and often poorl...

2015
Ayako Mizoguchi Yuki Hashimoto Yasuhiro Shinmei Mayo Nozaki Kan Ishijima Yoshiaki Tagawa Susumu Ishida

BACKGROUND Leber's hereditary optic neuropathy (LHON) refers to an optic nerve dysfunction due to mutations in the mitochondrial DNA, resulting in visual loss by apoptosis of retinal ganglion cells (RGC). In 20% of LHON cases, their fundus examination looks entirely normal at early stage. There are some reports regarding the circumpapillary retinal nerve fiber layer (cpRNFL) and the ganglion ce...

Journal: :Archives of neurology 2007
Liesbeth Spruijt Hubert J Smeets Alexandra Hendrickx Marijke Wefers Bettink-Remeijer A Maat-Kievit Kees C Schoonderwoerd Wim Sluiter Ireneaus F de Coo Rogier Q Hintzen

OBJECTIVE To report a novel mutation that is associated with Leber hereditary optic neuropathy (LHON) within the same family affected by spastic dystonia. DESIGN Leber hereditary optic neuropathy is a mitochondrial disorder characterized by isolated central visual loss. Of patients with LHON, 95% carry a mutation in 1 of 3 mitochondrial DNA-encoded complex I genes. The complete mitochondrial ...

2007
Valerio Carelli Flavia Franceschini Silvia Venturi Piero Barboni Giacomo Savini Giuseppe Barbieri Ettore Pirro Chiara La Morgia Maria L. Valentino Francesca Zanardi Francesco S. Violante Stefano Mattioli

CONTEXT Leber hereditary optic neuropathy (LHON) is a maternally inherited loss of central vision related to pathogenic mutations in the mitochondrial genome, which are a necessary but not sufficient condition to develop the disease. Investigation of precipitating environmental/occupational (and additional genetic) factors could be relevant for prevention. CASE PRESENTATION After a 6-month pe...

2011
Marcela Scabello Amaral-Fernandes Ana Maria Marcondes Paulo Maurício do Amor Divino Miranda Andréa Trevas Maciel-Guerra Edi Lúcia Sartorato

PURPOSE There are many similarities in the clinical presentation of Leber hereditary optic neuropathy (LHON) and in patients who have optic neuropathy and a history of heavy tobacco and alcohol consumption. The main objective of this study is to investigate the frequency of primary and secondary mitochondrial DNA (mtDNA) mutations for LHON in patients diagnosed as having alcohol and tobacco opt...

2013
Nahid Akhtar Khan Periyasamy Govindaraj Vuskamalla Jyothi Angamuthu K Meena Kumarasamy Thangaraj

BACKGROUND Mitochondrial DNA (mtDNA) mutations are known to cause Leber hereditary optic neuropathy (LHON). However, the co-occurrence of double pathogenic mutations with different pathological significance in pedigrees is a rare event. METHODS Detailed clinical investigation and complete mtDNA sequencing analysis was performed for two Indian families with LHON. The haplogroup was constructed...

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